Literature DB >> 15792865

An autosomal recessive limb girdle muscular dystrophy (LGMD2) with mild mental retardation is allelic to Walker-Warburg syndrome (WWS) caused by a mutation in the POMT1 gene.

Burcu Balci1, Gökhan Uyanik, Pervin Dincer, Claudia Gross, Tobias Willer, Beril Talim, Göknur Haliloglu, Gülsev Kale, Ute Hehr, Jürgen Winkler, Haluk Topaloğlu.   

Abstract

Mutations of the protein O-mannosyltransferase (POMT1) gene affect glycosylation of alpha-dystroglycan, leading to Walker-Warburg syndrome, a lethal disorder in early life with severe congenital muscular dystrophy, and brain and eye malformations. Recently, we described a novel form of recessive limb girdle muscular dystrophy with mild mental retardation, associated with an abnormal alpha-dystroglycan pattern in the muscle, suggesting a glycosylation defect. Here, we present evidence that this distinct phenotype results from a common mutation (A200P) in the POMT1 gene. Our findings further expand the phenotype of glycosylation disorders linked to POMT1 mutations. Furthermore, the A200P mutation is part of a conserved core haplotype, indicating an ancestral founder mutation.

Entities:  

Mesh:

Substances:

Year:  2005        PMID: 15792865     DOI: 10.1016/j.nmd.2005.01.013

Source DB:  PubMed          Journal:  Neuromuscul Disord        ISSN: 0960-8966            Impact factor:   4.296


  42 in total

1.  Evidence-based guideline summary: evaluation, diagnosis, and management of congenital muscular dystrophy: Report of the Guideline Development Subcommittee of the American Academy of Neurology and the Practice Issues Review Panel of the American Association of Neuromuscular & Electrodiagnostic Medicine.

Authors:  Peter B Kang; Leslie Morrison; Susan T Iannaccone; Robert J Graham; Carsten G Bönnemann; Anne Rutkowski; Joseph Hornyak; Ching H Wang; Kathryn North; Maryam Oskoui; Thomas S D Getchius; Julie A Cox; Erin E Hagen; Gary Gronseth; Robert C Griggs
Journal:  Neurology       Date:  2015-03-31       Impact factor: 9.910

Review 2.  Mechanisms of disease: congenital muscular dystrophies-glycosylation takes center stage.

Authors:  Paul T Martin
Journal:  Nat Clin Pract Neurol       Date:  2006-04

3.  Mammalian O-mannosylation of cadherins and plexins is independent of protein O-mannosyltransferases 1 and 2.

Authors:  Ida Signe Bohse Larsen; Yoshiki Narimatsu; Hiren Jitendra Joshi; Zhang Yang; Oliver J Harrison; Julia Brasch; Lawrence Shapiro; Barry Honig; Sergey Y Vakhrushev; Henrik Clausen; Adnan Halim
Journal:  J Biol Chem       Date:  2017-05-16       Impact factor: 5.157

Review 4.  The dystroglycanopathies: the new disorders of O-linked glycosylation.

Authors:  Paul T Martin
Journal:  Semin Pediatr Neurol       Date:  2005-09       Impact factor: 1.636

5.  Muscular dystrophy associated with alpha-dystroglycan deficiency in Sphynx and Devon Rex cats.

Authors:  Paul T Martin; G Diane Shelton; Peter J Dickinson; Beverly K Sturges; Rui Xu; Richard A LeCouteur; Ling T Guo; Robert A Grahn; Harriet P Lo; Kathryn N North; Richard Malik; Eva Engvall; Leslie A Lyons
Journal:  Neuromuscul Disord       Date:  2008-11-05       Impact factor: 4.296

6.  Analysis of phenotype, enzyme activity and genotype of Chinese patients with POMT1 mutation.

Authors:  Haipo Yang; Hiroshi Manya; Kazuhiro Kobayashi; Hui Jiao; Xiaona Fu; Jiangxi Xiao; Xiaoqing Li; Jingmin Wang; Yuwu Jiang; Tatsushi Toda; Tamao Endo; Xiru Wu; Hui Xiong
Journal:  J Hum Genet       Date:  2016-05-19       Impact factor: 3.172

7.  Expression of the murine Pomt1 gene in both the developing brain and adult muscle tissues and its relationship with clinical aspects of Walker-Warburg syndrome.

Authors:  Belén Prados; Almudena Peña; Rocío P Cotarelo; M Carmen Valero; Jesús Cruces
Journal:  Am J Pathol       Date:  2007-05       Impact factor: 4.307

8.  Identification of mutations in TMEM5 and ISPD as a cause of severe cobblestone lissencephaly.

Authors:  Sandrine Vuillaumier-Barrot; Céline Bouchet-Séraphin; Malika Chelbi; Louise Devisme; Samuel Quentin; Steven Gazal; Annie Laquerrière; Catherine Fallet-Bianco; Philippe Loget; Sylvie Odent; Dominique Carles; Anne Bazin; Jacqueline Aziza; Alix Clemenson; Fabien Guimiot; Maryse Bonnière; Sophie Monnot; Christine Bole-Feysot; Jean-Pierre Bernard; Laurence Loeuillet; Marie Gonzales; Koryna Socha; Bernard Grandchamp; Tania Attié-Bitach; Férechté Encha-Razavi; Nathalie Seta
Journal:  Am J Hum Genet       Date:  2012-12-07       Impact factor: 11.025

9.  Atypical manifestation of late onset limb girdle muscular dystrophy presenting with recurrent falling and shoulder dysfunction: a case report.

Authors:  Markus Dietmar Schofer; Thilo Patzer; Markus Quante
Journal:  Cases J       Date:  2008-12-16

Review 10.  The roles of the dystrophin-associated glycoprotein complex at the synapse.

Authors:  Gonneke S K Pilgram; Saranyapin Potikanond; Richard A Baines; Lee G Fradkin; Jasprina N Noordermeer
Journal:  Mol Neurobiol       Date:  2009-11-09       Impact factor: 5.590

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.