| Literature DB >> 12776252 |
Nazneen Rahman1, Melanie Dunstan, M Dawn Teare, Sandra Hanks, Jenny Douglas, Kim Coleman, William E Bottomly, Mary E Campbell, Britta Berglund, Magnus Nordenskjöld, Bengt Forssell, Nigel Burrows, Peter Lunt, Ian Young, Nigel Williams, Graham R Bignell, P Andrew Futreal, F Michael Pope.
Abstract
Ehlers-Danlos VIII (EDS-VIII) is an autosomal dominant disorder characterized by severe early-onset periodontal disease in conjunction with the features of Ehlers-Danlos syndrome (EDS). We performed a genomewide linkage search in a large Swedish pedigree with EDS-VIII and established linkage to a 7-cM interval on chromosome 12p13, generating a maximum multipoint LOD score of 5.17. Analysis of four further pedigrees with EDS-VIII revealed two consistent with linkage to 12p13 and two in which linkage could be excluded, indicating that EDS-VIII is a genetically heterogeneous disorder. Chromosome 12p13 has not previously been implicated in either EDS or periodontal disease and contains no known collagen genes or collagen-processing enzymes. Mutational screening of the microfibril-associated glycoprotein-2 gene, a strong candidate within the minimal interval, did not reveal any likely pathogenic mutations.Entities:
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Year: 2003 PMID: 12776252 PMCID: PMC1180581 DOI: 10.1086/376416
Source DB: PubMed Journal: Am J Hum Genet ISSN: 0002-9297 Impact factor: 11.025