Literature DB >> 12107518

Prevalence and geographical distribution of Usher syndrome in Germany.

Ulrich H M Spandau1, Klaus Rohrschneider.   

Abstract

PURPOSE: To estimate the prevalence of Usher syndrome in Heidelberg and Mannheim and to map its geographical distribution in Germany.
METHODS: Usher syndrome patients were ascertained through the databases of the Low Vision Department at the University of Heidelberg, and of the patient support group Pro Retina. Ophthalmic and audiologic examinations and medical records were used to classify patients into one of the subtypes.
RESULTS: The database of the University of Heidelberg contains 247 Usher syndrome patients, 63 with Usher syndrome type 1 (USH1) and 184 with Usher syndrome type 2 (USH2). The USH1:USH2 ratio in the Heidelberg database was 1:3. The Pro Retina database includes 248 Usher syndrome patients, 21 with USH1 and 227 with USH2. The total number of Usher syndrome patients was 424, with 75 USH1 and 349 USH2 patients; 71 patients were in both databases. The prevalence of Usher syndrome in Heidelberg and suburbs was calculated to be 6.2 per 100,000 inhabitants. There seems to be a homogeneous distribution in Germany for both subtypes.
CONCLUSION: Knowledge of the high prevalence of Usher syndrome, with up to 5,000 patients in Germany, should lead to increased awareness and timely diagnosis by ophthalmologists and otologists. It should also ensure that these patients receive good support through hearing and vision aids.

Entities:  

Mesh:

Year:  2002        PMID: 12107518     DOI: 10.1007/s00417-002-0485-8

Source DB:  PubMed          Journal:  Graefes Arch Clin Exp Ophthalmol        ISSN: 0721-832X            Impact factor:   3.117


  31 in total

Review 1.  Genetics and pathological mechanisms of Usher syndrome.

Authors:  Denise Yan; Xue Z Liu
Journal:  J Hum Genet       Date:  2010-04-09       Impact factor: 3.172

2.  Novel mutations in the long isoform of the USH2A gene in patients with Usher syndrome type II or non-syndromic retinitis pigmentosa.

Authors:  Terri L McGee; Babak Jian Seyedahmadi; Meredith O Sweeney; Thaddeus P Dryja; Eliot L Berson
Journal:  J Med Genet       Date:  2010-05-27       Impact factor: 6.318

3.  Mutational screening of the USH2A gene in Spanish USH patients reveals 23 novel pathogenic mutations.

Authors:  Gema Garcia-Garcia; Maria J Aparisi; Teresa Jaijo; Regina Rodrigo; Ana M Leon; Almudena Avila-Fernandez; Fiona Blanco-Kelly; Sara Bernal; Rafael Navarro; Manuel Diaz-Llopis; Montserrat Baiget; Carmen Ayuso; Jose M Millan; Elena Aller
Journal:  Orphanet J Rare Dis       Date:  2011-10-17       Impact factor: 4.123

4.  A novel gene for Usher syndrome type 2: mutations in the long isoform of whirlin are associated with retinitis pigmentosa and sensorineural hearing loss.

Authors:  Inga Ebermann; Hendrik P N Scholl; Peter Charbel Issa; Elvir Becirovic; Jürgen Lamprecht; Bernhard Jurklies; José M Millán; Elena Aller; Diana Mitter; Hanno Bolz
Journal:  Hum Genet       Date:  2006-12-15       Impact factor: 4.132

5.  Children with Usher syndrome: mental and behavioral disorders.

Authors:  Jesper Dammeyer
Journal:  Behav Brain Funct       Date:  2012-03-27       Impact factor: 3.759

6.  The expression of whirlin and Cav1.3α₁ is mutually independent in photoreceptors.

Authors:  Junhuang Zou; Amy Lee; Jun Yang
Journal:  Vision Res       Date:  2012-08-07       Impact factor: 1.886

7.  Usher syndrome and Leber congenital amaurosis are molecularly linked via a novel isoform of the centrosomal ninein-like protein.

Authors:  Erwin van Wijk; Ferry F J Kersten; Aileen Kartono; Dorus A Mans; Kim Brandwijk; Stef J F Letteboer; Theo A Peters; Tina Märker; Xiumin Yan; Cor W R J Cremers; Frans P M Cremers; Uwe Wolfrum; Ronald Roepman; Hannie Kremer
Journal:  Hum Mol Genet       Date:  2008-09-30       Impact factor: 6.150

8.  An epidemiological approach for the estimation of disease onset in Central Europe in central and peripheral monogenic retinal dystrophies.

Authors:  Elena Prokofyeva; Robert Wilke; Gunnar Lotz; Eric Troeger; Torsten Strasser; Eberhart Zrenner
Journal:  Graefes Arch Clin Exp Ophthalmol       Date:  2009-03-11       Impact factor: 3.117

9.  Identification of 51 novel exons of the Usher syndrome type 2A (USH2A) gene that encode multiple conserved functional domains and that are mutated in patients with Usher syndrome type II.

Authors:  Erwin van Wijk; Ronald J E Pennings; Heleen te Brinke; Annemarie Claassen; Helger G Yntema; Lies H Hoefsloot; Frans P M Cremers; Cor W R J Cremers; Hannie Kremer
Journal:  Am J Hum Genet       Date:  2004-03-10       Impact factor: 11.025

10.  Disease-causing mutations in the CLRN1 gene alter normal CLRN1 protein trafficking to the plasma membrane.

Authors:  Juha Isosomppi; Hanna Västinsalo; Scott F Geller; Elise Heon; John G Flannery; Eeva-Marja Sankila
Journal:  Mol Vis       Date:  2009-09-08       Impact factor: 2.367

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