| Literature DB >> 11313956 |
L D Wood1, T L Halvorsen, S Dhar, J A Baur, R K Pandita, W E Wright, M P Hande, G Calaf, T K Hei, F Levine, J W Shay, J J Wang, T K Pandita.
Abstract
Ataxia-telangiectasia (A-T) is an autosomal recessive disease characterized by progressive cerebellar degeneration, immunodeficiencies, genomic instability and gonadal atrophy. A-T patients are hypersensitive to ionizing radiation and have an elevated cancer risk. Cells derived from A-T patients require higher levels of serum factors, exhibit cytoskeletal defects and undergo premature senescence in culture. We show here that expression of the catalytic subunit of telomerase (hTERT) in primary A-T patient fibroblasts can rescue the premature senescence phenotype. Ectopic expression of hTERT does not rescue the radiosensitivity or the telomere fusions in A-T fibroblasts. The hTERT+AT cells also retain the characteristic defects in cell-cycle checkpoints, and show increased chromosome damage before and after ionizing radiation. Although A-T patients have an increased susceptibility to cancer, the expression of hTERT in A-T fibroblasts does not stimulate malignant transformation. These immortalized A-T cells provide a more stable cell system to investigate the molecular mechanisms underlying the cellular phenotypes of Ataxia-telangiectasia.Entities:
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Year: 2001 PMID: 11313956 DOI: 10.1038/sj.onc.1204072
Source DB: PubMed Journal: Oncogene ISSN: 0950-9232 Impact factor: 9.867