Literature DB >> 9677071

X-linked dominant chondrodysplasia punctata: a peroxisomal disorder?

C J Wilson1, S Aftimos.   

Abstract

X-linked dominant chondrodysplasia punctata is characterised by resolving irregular punctate calcifications of epiphyses, variable ichthyosis and atrophoderma, short stature, and cataracts. We report on a patient with this syndrome who had transiently abnormal peroxisomal function tests. We review the literature and propose that X-linked dominant chondrodysplasia punctata is a peroxisomal disorder and that its phenotype can be explained by X chromosome lyonisation and the relative proliferation of cells expressing the normal X allele.

Entities:  

Mesh:

Year:  1998        PMID: 9677071     DOI: 10.1002/(sici)1096-8628(19980707)78:3<300::aid-ajmg19>3.0.co;2-j

Source DB:  PubMed          Journal:  Am J Med Genet        ISSN: 0148-7299


  2 in total

Review 1.  Pathogenesis of permeability barrier abnormalities in the ichthyoses: inherited disorders of lipid metabolism.

Authors:  Peter M Elias; Mary L Williams; Walter M Holleran; Yan J Jiang; Matthias Schmuth
Journal:  J Lipid Res       Date:  2008-02-02       Impact factor: 5.922

2.  Pathogenesis of the cutaneous phenotype in inherited disorders of cholesterol metabolism: Therapeutic implications for topical treatment of these disorders.

Authors:  Peter M Elias; Debra Crumrine; Amy Paller; Marina Rodriguez-Martin; Mary L Williams
Journal:  Dermatoendocrinol       Date:  2011-04-01
  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.