Literature DB >> 9445373

Analysis of abnormalities in purine metabolism leading to gout and to neurological dysfunctions in man.

R Curto1, E O Voit, M Cascante.   

Abstract

A modelling approach is used to analyse diseases associated with purine metabolism in man. The specific focus is on deficiencies in two enzymes, hypoxanthine:guanine phosphoribosyltransferase and adenylosuccinate lyase. These deficiencies can lead to a number of symptoms, including neurological dysfunctions and mental retardation. Although the biochemical mechanisms of dysfunctions associated with adenylosuccinate lyase deficiency are not completely understood, there is at least general agreement in the literature about possible causes. Simulations with our model confirm that accumulation of the two substrates of the enzyme can lead to significant biochemical imbalance. In hypoxanthine:guanine phosphoribosyltransferase deficiency the biochemical mechanisms associated with neurological dysfunctions are less clear. Model analyses support some old hypotheses but also suggest new indicators for possible causes of neurological dysfunctions associated with this deficiency. Hypoxanthine:guanine phosphoribosyltransferase deficiency is known to cause hyperuricaemia and gout. We compare the relative importance of this deficiency with other known causes of gout in humans. The analysis suggests that defects in the excretion of uric acid are more consequential than defects in uric acid synthesis such as hypoxanthine:guanine phosphoribosyltransferase deficiency.

Entities:  

Mesh:

Substances:

Year:  1998        PMID: 9445373      PMCID: PMC1219067          DOI: 10.1042/bj3290477

Source DB:  PubMed          Journal:  Biochem J        ISSN: 0264-6021            Impact factor:   3.857


  38 in total

1.  Nucleotide requirement of dopamine sensitive adenylate cyclase in synaptosomal membranes from the striatum of rat brain.

Authors:  B D Roufogalis; M Thornton; D N Wade
Journal:  J Neurochem       Date:  1976-12       Impact factor: 5.372

2.  IMP dehydrogenase, an enzyme linked with proliferation and malignancy.

Authors:  R C Jackson; G Weber; H P Morris
Journal:  Nature       Date:  1975-07-24       Impact factor: 49.962

3.  Hypoxanthine-guanine phosphoribosyltransferase deficiency: altered kinetic properties of a specific mutant form of the enzyme.

Authors:  J A McDonald; W N Kelley
Journal:  Adv Exp Med Biol       Date:  1973       Impact factor: 2.622

Review 4.  Hypoxanthine-guanine phosphoribosyltransferase deficiency in gout.

Authors:  W N Kelley; M L Greene; F M Rosenbloom; J F Henderson; J E Seegmiller
Journal:  Ann Intern Med       Date:  1969-01       Impact factor: 25.391

5.  Partial deficiency of hypoxanthine-guanine phosphoribosyltransferase associated with gout and uric acid lithiasis.

Authors:  O Sperling; M Frank; R Ophir; U A Liberman; A Adam; A de Vries
Journal:  Rev Eur Etud Clin Biol       Date:  1970-11

6.  Validation and steady-state analysis of a power-law model of purine metabolism in man.

Authors:  R Curto; E O Voit; A Sorribas; M Cascante
Journal:  Biochem J       Date:  1997-06-15       Impact factor: 3.857

7.  Kinetic, physical, and regulatory properties of amidophosphoribosyltransferase.

Authors:  E W Holmes
Journal:  Adv Enzyme Regul       Date:  1980

8.  Lesch-Nyhan syndrome: low dopamine-beta-hydroxylase activity and diminished sympathetic response to stress and posture.

Authors:  C R Lake; M G Ziegler
Journal:  Science       Date:  1977-05-20       Impact factor: 47.728

9.  Observations on the growth in vitro of myeloid progenitor cells and fibroblasts from hemizygotes and heterozygotes for "complete" and "partial" hypoxanthine-guanine phosphoribosyltransferase (HGPRT) deficiency, and their relevance to the pathogenesis of brain damage in the Lesch-Nyhan syndrome.

Authors:  R O McKeran; A Howell; T M Andrews; R W Watts; C F Arlett
Journal:  J Neurol Sci       Date:  1974-06       Impact factor: 3.181

10.  Lesch-Nyhan syndrome: altered kinetic properties of mutant enzyme.

Authors:  J A McDonald; W N Kelley
Journal:  Science       Date:  1971-02-19       Impact factor: 47.728

View more
  17 in total

1.  Strategies for Comparing Metabolic Profiles: Implications for the Inference of Biochemical Mechanisms from Metabolomics Data.

Authors:  Zhen Qi; Eberhard O Voit
Journal:  IEEE/ACM Trans Comput Biol Bioinform       Date:  2016-07-07       Impact factor: 3.710

Review 2.  Biological systems modeling and analysis: a biomolecular technique of the twenty-first century.

Authors:  Gautam Goel; I-Chun Chou; Eberhard O Voit
Journal:  J Biomol Tech       Date:  2006-09

3.  Do clinical features of Lesch-Nyhan disease correlate more closely with hypoxanthine or guanine recycling?

Authors:  David J Schretlen; Wynne Callon; Rebecca E Ward; Rong Fu; Tiffany Ho; Barry Gordon; James C Harris; H A Jinnah
Journal:  J Inherit Metab Dis       Date:  2015-06-12       Impact factor: 4.982

Review 4.  Dynamical systems approaches to personalized medicine.

Authors:  Jacob D Davis; Carla M Kumbale; Qiang Zhang; Eberhard O Voit
Journal:  Curr Opin Biotechnol       Date:  2019-04-09       Impact factor: 9.740

5.  Genotype-phenotype correlations in Lesch-Nyhan disease: moving beyond the gene.

Authors:  Rong Fu; H A Jinnah
Journal:  J Biol Chem       Date:  2011-12-07       Impact factor: 5.157

6.  Metabolic modeling helps interpret transcriptomic changes during malaria.

Authors:  Yan Tang; Anuj Gupta; Swetha Garimalla; Mary R Galinski; Mark P Styczynski; Luis L Fonseca; Eberhard O Voit
Journal:  Biochim Biophys Acta Mol Basis Dis       Date:  2017-10-22       Impact factor: 5.187

Review 7.  A systems-theoretical framework for health and disease: inflammation and preconditioning from an abstract modeling point of view.

Authors:  Eberhard O Voit
Journal:  Math Biosci       Date:  2008-09-27       Impact factor: 2.144

8.  Tuna extract reduces serum uric acid in gout-free subjects with insignificantly high serum uric acid: A randomized controlled trial.

Authors:  Daiki Kubomura; Masanori Yamada; Ayano Masui
Journal:  Biomed Rep       Date:  2016-06-09

Review 9.  Recent developments in parameter estimation and structure identification of biochemical and genomic systems.

Authors:  I-Chun Chou; Eberhard O Voit
Journal:  Math Biosci       Date:  2009-03-25       Impact factor: 2.144

10.  Identification of cancer mechanisms through computational systems modeling.

Authors:  Zhen Qi; Eberhard O Voit
Journal:  Transl Cancer Res       Date:  2014-06-01       Impact factor: 1.241

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.