Literature DB >> 9365070

Cerebral complications in Schimke immuno-osseous dysplasia.

B Schmidt1, H J Christen, P Herkenrath, G Benz-Bohm, J Müller-Berghaus, U Querfeld.   

Abstract

UNLABELLED: Schimke immuno-osseous dysplasia is a multisystem disorder consisting of spondylo-epiphysial dysplasia, progressive renal insufficiency due to focal segmental glomerulosclerosis, and immunodeficiency. Cerebrovascular complications have only been described in five patients. Here we report a patient with prominent neurological symptoms most likely caused by transient ischaemic attacks.
CONCLUSION: Neurological symptoms consisted of repeated brief spells of hemiparaesthesia, motoric aphasia and diplopia. MRI studies of the CNS revealed progressive white matter lesions. Morphological changes as well as neurological deficits are compatible with cerebral ischaemia.

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Year:  1997        PMID: 9365070     DOI: 10.1007/s004310050714

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  8 in total

1.  Pulmonary embolism--a rare complication of Schimke immunoosseous dysplasia.

Authors:  K Sauerstein; M Schroth; K Amann; J Hoyer; H Singer; A Rauch; J Dötsch
Journal:  Eur J Pediatr       Date:  2006-12-29       Impact factor: 3.183

2.  Reversible cerebral vasoconstriction complicating cerebral atherosclerotic vascular disease in Schimke immuno-osseous dysplasia.

Authors:  Mariasavina Severino; Thea Giacomini; Enrico Verrina; Giulia Prato; Andrea Rossi
Journal:  Neuroradiology       Date:  2018-07-06       Impact factor: 2.804

3.  Anesthetic management of Schimke syndrome.

Authors:  Ciğdem Yıldırım Güçlü; Ozlem Selvi Can; Menekşe Ozçelik
Journal:  J Anesth       Date:  2014-01-29       Impact factor: 2.078

4.  Insights into the renal pathogenesis in Schimke immuno-osseous dysplasia: A renal histological characterization and expression analysis.

Authors:  Sanjay Sarin; Ashkan Javidan; Felix Boivin; Iakovina Alexopoulou; Dusan Lukic; Bruno Svajger; Stephanie Chu; Alireza Baradaran-Heravi; Cornelius F Boerkoel; Norman D Rosenblum; Darren Bridgewater
Journal:  J Histochem Cytochem       Date:  2014-10-15       Impact factor: 2.479

5.  Mitochondrial function in schimke-immunoosseous dysplasia.

Authors:  Thomas Lücke; Jochen H H Ehrich; Anibh M Das
Journal:  Metab Brain Dis       Date:  2005-09       Impact factor: 3.584

6.  Schimke immuno-osseous dysplasia: a clinicopathological correlation.

Authors:  J Marietta Clewing; Barbara C Antalfy; Thomas Lücke; Behzad Najafian; Katja M Marwedel; Akira Hori; Ralph M Powel; A F Safo Do; Lydia Najera; Karen SantaCruz; M John Hicks; Dawna L Armstrong; Corndins F Boerkoel
Journal:  J Med Genet       Date:  2006-07-13       Impact factor: 6.318

7.  Generalized atherosclerosis sparing the transplanted kidney in Schimke disease.

Authors:  Thomas Lücke; Katja M Marwedel; Nele K Kanzelmeyer; Akira Hori; Gisela Offner; Hans-Heinrich Kreipe; Jochen H H Ehrich; Anibh M Das
Journal:  Pediatr Nephrol       Date:  2004-03-31       Impact factor: 3.714

8.  Schimke immunoosseous dysplasia: defining skeletal features.

Authors:  Kshamta B Hunter; Thomas Lücke; Jürgen Spranger; Sarah F Smithson; Harika Alpay; Jean-Luc André; Yumi Asakura; Radovan Bogdanovic; Dominique Bonneau; Robyn Cairns; Karlien Cransberg; Stefan Fründ; Helen Fryssira; David Goodman; Knut Helmke; Barbara Hinkelmann; Guiliana Lama; Petra Lamfers; Chantal Loirat; Silvia Majore; Christy Mayfield; Bertram F Pontz; Cristina Rusu; Jorge M Saraiva; Beate Schmidt; Lawrence Shoemaker; Sabine Sigaudy; Natasa Stajic; Doris Taha; Cornelius F Boerkoel
Journal:  Eur J Pediatr       Date:  2009-12-15       Impact factor: 3.183

  8 in total

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