| Literature DB >> 9335046 |
R M Petters1, C A Alexander, K D Wells, E B Collins, J R Sommer, M R Blanton, G Rojas, Y Hao, W L Flowers, E Banin, A V Cideciyan, S G Jacobson, F Wong.
Abstract
Patients with retinitis pigmentosa (RP) typically develop night blindness early in life due to loss of rod photoreceptors. The remaining cone photoreceptors are the mainstay of their vision; however, over years or decades, these cones slowly degenerate, leading to blindness. We created transgenic pigs that express a mutated rhodopsin gene (Pro347Leu). Like RP patients with the same mutation, these pigs have early and severe rod loss; initially their cones are relatively spared, but these surviving cones slowly degenerate. By age 20 months, there is only a single layer of morphologically abnormal cones and the cone electroretinogram is markedly reduced. Given the strong similarities in phenotype to that of RP patients, these transgenic pigs will provide a large animal model for study of the protracted phase of cone degeneration found in RP and for preclinical treatment trials.Entities:
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Year: 1997 PMID: 9335046 DOI: 10.1038/nbt1097-965
Source DB: PubMed Journal: Nat Biotechnol ISSN: 1087-0156 Impact factor: 54.908