Literature DB >> 9296536

An asymptomatic infant with isolated 3-methylcrotonyl-coenzyme: a carboxylase deficiency detected by newborn screening for maple syrup urine disease.

K Ihara1, R Kuromaru, Y Inoue, T Kuhara, I Matsumoto, M Yoshino, J Fukushige.   

Abstract

UNLABELLED: We describe an asymptomatic male infant with isolated 3-methylcrotonyl-coenzyme A carboxylase deficiency who came to medical attention by newborn mass screening due to elevated blood leucine. The diagnosis was made by abnormal urinary organic acids at 20 days of age and was confirmed by assay of the carboxylase activities in cultured skin fibroblasts.
CONCLUSION: More attention should be paid to slight elevations of leucine levels in newborn mass screening. Urinary organic acid analysis should be performed in conspicuous cases.

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Year:  1997        PMID: 9296536     DOI: 10.1007/s004310050696

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  4 in total

1.  The diagnosis and management of patients with idiopathic osteolysis.

Authors:  Ali Al Kaissi; Sabine Scholl-Buergi; Rainer Biedermann; Kathrin Maurer; Jochen G Hofstaetter; Klaus Klaushofer; Franz Grill
Journal:  Pediatr Rheumatol Online J       Date:  2011-10-13       Impact factor: 3.054

2.  Evaluation of 3-methylcrotonyl-CoA carboxylase deficiency detected by tandem mass spectrometry newborn screening.

Authors:  D D Koeberl; D S Millington; W E Smith; S D Weavil; J Muenzer; S E McCandless; P S Kishnani; M T McDonald; S Chaing; A Boney; E Moore; D M Frazier
Journal:  J Inherit Metab Dis       Date:  2003       Impact factor: 4.982

3.  Novel mutations in five Japanese patients with 3-methylcrotonyl-CoA carboxylase deficiency.

Authors:  Mitsugu Uematsu; Osamu Sakamoto; Noriko Sugawara; Naonori Kumagai; Tetsuji Morimoto; Seiji Yamaguchi; Yuki Hasegawa; Hironori Kobayashi; Kenji Ihara; Makoto Yoshino; Yoriko Watanabe; Takahiro Inokuchi; Takato Yokoyama; Kohji Kiwaki; Kimitoshi Nakamura; Fumio Endo; Shigeru Tsuchiya; Toshihiro Ohura
Journal:  J Hum Genet       Date:  2007-10-30       Impact factor: 3.172

4.  3-methylcrotonyl-CoA carboxylase deficiency: clinical, biochemical, enzymatic and molecular studies in 88 individuals.

Authors:  Sarah C Grünert; Martin Stucki; Raphael J Morscher; Terttu Suormala; Celine Bürer; Patricie Burda; Ernst Christensen; Can Ficicioglu; Jürgen Herwig; Stefan Kölker; Dorothea Möslinger; Elisabetta Pasquini; René Santer; K Otfried Schwab; Bridget Wilcken; Brian Fowler; Wyatt W Yue; Matthias R Baumgartner
Journal:  Orphanet J Rare Dis       Date:  2012-05-29       Impact factor: 4.123

  4 in total

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