Literature DB >> 9266388

Identification of 'private' mutations in patients with ornithine transcarbamylase deficiency.

M Tuchman1, H Morizono, B S Rajagopal, R J Plante, N M Allewell.   

Abstract

The majority of cases of ornithine transcarbamylase deficiency are due to novel mutations making it impossible to develop common methods for genetic analysis. However, identification of causative mutations has important implications for diagnosis (particularly prenatal diagnosis), prediction of likely course and outcome and the eventual possibility of gene therapy. As part of a continuing study of ornithine transcarbamylase deficiency, we now report an additional thirty novel mutations in the ornithine transcarbamylase gene, together with a brief summary of their clinical presentations.

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Year:  1997        PMID: 9266388     DOI: 10.1023/a:1005301513465

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  4 in total

1.  Relative frequency of mutations causing ornithine transcarbamylase deficiency in 78 families.

Authors:  M Tuchman; R J Plante; M A Garcia-Perez; V Rubio
Journal:  Hum Genet       Date:  1996-03       Impact factor: 4.132

Review 2.  Mutations and polymorphisms in the human ornithine transcarbamylase gene.

Authors:  M Tuchman
Journal:  Hum Mutat       Date:  1993       Impact factor: 4.878

3.  The molecular basis of ornithine transcarbamylase deficiency: modelling the human enzyme and the effects of mutations.

Authors:  M Tuchman; H Morizono; O Reish; X Yuan; N M Allewell
Journal:  J Med Genet       Date:  1995-09       Impact factor: 6.318

Review 4.  Mutations and polymorphisms in the human ornithine transcarbamylase gene: mutation update addendum.

Authors:  M Tuchman; R J Plante
Journal:  Hum Mutat       Date:  1995       Impact factor: 4.878

  4 in total
  14 in total

1.  Prenatal molecular diagnosis of severe ornithine carbamoyltransferase deficiency due to a novel mutation, E181G.

Authors:  A K Topaloglu; C Sansaricq; J E Fox; A E Bale; M Tuchman; R J Desnick
Journal:  J Inherit Metab Dis       Date:  1999-02       Impact factor: 4.982

2.  Substrate-induced conformational change in a trimeric ornithine transcarbamoylase.

Authors:  Y Ha; M T McCann; M Tuchman; N M Allewell
Journal:  Proc Natl Acad Sci U S A       Date:  1997-09-02       Impact factor: 11.205

3.  Two novel mutations of ornithine transcarbamylase gene identified from three Chinese neonates with ornithine transcarbamylase deficiency.

Authors:  Jing Liu; Lei Dong; Yan Wang; Mei Zhang
Journal:  Int J Clin Exp Med       Date:  2015-02-15

4.  Clinical outcomes and the mutation spectrum of the OTC gene in patients with ornithine transcarbamylase deficiency.

Authors:  Jin-Ho Choi; Beom Hee Lee; Ja Hye Kim; Gu-Hwan Kim; Yoo-Mi Kim; Jahyang Cho; Chong-Kun Cheon; Jung Min Ko; Jung Hyun Lee; Han-Wook Yoo
Journal:  J Hum Genet       Date:  2015-09       Impact factor: 3.172

Review 5.  Genotype-Phenotype Correlations in Ornithine Transcarbamylase Deficiency: A Mutation Update.

Authors:  Ljubica Caldovic; Iman Abdikarim; Sahas Narain; Mendel Tuchman; Hiroki Morizono
Journal:  J Genet Genomics       Date:  2015-05-19       Impact factor: 4.275

6.  In vivo urea cycle flux distinguishes and correlates with phenotypic severity in disorders of the urea cycle.

Authors:  B Lee; H Yu; F Jahoor; W O'Brien; A L Beaudet; P Reeds
Journal:  Proc Natl Acad Sci U S A       Date:  2000-07-05       Impact factor: 11.205

7.  Complex management of a patient with a contiguous Xp11.4 gene deletion involving ornithine transcarbamylase: a role for detailed molecular analysis in complex presentations of classical diseases.

Authors:  Matthew A Deardorff; Himabindu Gaddipati; Paige Kaplan; Pedro A Sanchez-Lara; Neal Sondheimer; Nancy B Spinner; Hakon Hakonarson; Can Ficicioglu; Jaya Ganesh; Thomas Markello; Brett Loechelt; Dina J Zand; Marc Yudkoff; Uta Lichter-Konecki
Journal:  Mol Genet Metab       Date:  2008-06-03       Impact factor: 4.797

8.  Estimation of the total number of disease-causing mutations in ornithine transcarbamylase (OTC) deficiency. Value of the OTC structure in predicting a mutation pathogenic potential.

Authors:  J A Arranz; E Riudor; C Marco-Marín; V Rubio
Journal:  J Inherit Metab Dis       Date:  2007-03-01       Impact factor: 4.750

9.  Frequency and Pathophysiology of Acute Liver Failure in Ornithine Transcarbamylase Deficiency (OTCD).

Authors:  Alexander Laemmle; Renata C Gallagher; Adrian Keogh; Tamar Stricker; Matthias Gautschi; Jean-Marc Nuoffer; Matthias R Baumgartner; Johannes Häberle
Journal:  PLoS One       Date:  2016-04-12       Impact factor: 3.240

10.  Urea cycle disorders in India: clinical course, biochemical and genetic investigations, and prenatal testing.

Authors:  Sunita Bijarnia-Mahay; Johannes Häberle; Anil B Jalan; Ratna Dua Puri; Sudha Kohli; Ketki Kudalkar; Véronique Rüfenacht; Deepti Gupta; Deepshikha Maurya; Jyotsna Verma; Yosuke Shigematsu; Seiji Yamaguchi; Renu Saxena; Ishwar C Verma
Journal:  Orphanet J Rare Dis       Date:  2018-10-01       Impact factor: 4.123

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