Literature DB >> 8777926

Acromicric dysplasia and geleophysic dysplasia: similarities and differences.

R C Hennekam1, Y van Bever, J W Oorthuys.   

Abstract

UNLABELLED: We report on a girl with severe growth retardation, characteristic facies, short stubby hands and feet, progressive joint stiffness, mild aortic and mitral valve insufficiency, and normal intelligence. These features are compatible with the diagnosis acromicric dysplasia. The differential diagnosis with Moore-Federman syndrome and geleophysic dysplasia is discussed; major points to consider in differentiating these entities are the facial appearance, the aspect of the proximal femora, and the presence or absence of storage phenomena. The differences in pattern of inheritance are important in adequate patient care, especially in genetic counselling.
CONCLUSION: Acromicric dysplasia, geleophysic dysplasia, and Moore-Federman syndrome may be allelic forms of the same disorder or different disturbances of the same metabolic pathway.

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Year:  1996        PMID: 8777926     DOI: 10.1007/bf02002719

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  11 in total

1.  FAMILIAL DWARFISM AND "STIFF JOINTS".

Authors:  W T MOORE; D D FEDERMAN
Journal:  Arch Intern Med       Date:  1965-04

2.  Mitral stenosis in an atypical case of gargoylism: a case report with pathologic and histochemical studies of the cardiac tissues.

Authors:  P W VANACE; S FRIEDMAN; B M WAGNER
Journal:  Circulation       Date:  1960-01       Impact factor: 29.690

3.  Geleophysic dwarfism--a "focal" mucopolysaccharidosis?

Authors:  J W Spranger; E F Gilbert; G A Tuffli; F P Rossiter; J M Opitz
Journal:  Lancet       Date:  1971-07-10       Impact factor: 79.321

4.  Reviving the Moore-Federman syndrome.

Authors:  J M Fell; R Stanhope
Journal:  J R Soc Med       Date:  1993-01       Impact factor: 5.344

5.  Geleophysic dysplasia.

Authors:  J Spranger; E F Gilbert; S Arya; G M Hoganson; J M Opitz
Journal:  Am J Med Genet       Date:  1984-11

6.  Moore-Federman syndrome and acromicric dysplasia: are they the same entity?

Authors:  R M Winter; M A Patton; J Challener; R F Mueller; M Baraitser
Journal:  J Med Genet       Date:  1989-05       Impact factor: 6.318

7.  Geleophysic dysplasia: a storage disorder affecting the skin, bone, liver, heart, and trachea.

Authors:  M Shohat; H E Gruber; R A Pagon; L J Witcoff; R Lachman; D Ferry; E Flaum; D L Rimoin
Journal:  J Pediatr       Date:  1990-08       Impact factor: 4.406

8.  Geleophysic dysplasia--acromicric dysplasia with evidence of glycoprotein storage.

Authors:  A H Lipson; A E Kan; K Kozlowski
Journal:  Am J Med Genet Suppl       Date:  1987

9.  Familial recurrence of geleophysic dysplasia.

Authors:  C P Koiffmann; A Wajntal; M J Ursich; A A Pupo
Journal:  Am J Med Genet       Date:  1984-11

10.  Acromicric dysplasia.

Authors:  P Maroteaux; R Stanescu; V Stanescu; R Rappaport
Journal:  Am J Med Genet       Date:  1986-07
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  3 in total

1.  Three novel mutations of the FBN1 gene in Chinese children with acromelic dysplasia.

Authors:  Yu Wang; Huiwen Zhang; Jun Ye; Lianshu Han; Xuefan Gu
Journal:  J Hum Genet       Date:  2014-08-21       Impact factor: 3.172

2.  Acromicric dysplasia: long term outcome and evidence of autosomal dominant inheritance.

Authors:  L Faivre; M Le Merrer; C Baumann; M Polak; P Chatelain; V Sulmont; J Cousin; M Bost; M P Cordier; E Zackai; K Russell; G Finidori; J C Pouliquen; A Munnich; P Maroteaux; V Cormier-Daire
Journal:  J Med Genet       Date:  2001-11       Impact factor: 6.318

3.  Molecular screening of ADAMTSL2 gene in 33 patients reveals the genetic heterogeneity of geleophysic dysplasia.

Authors:  Slimane Allali; Carine Le Goff; Isabelle Pressac-Diebold; Gwendoline Pfennig; Clémentine Mahaut; Nathalie Dagoneau; Yasemin Alanay; Angela F Brady; Yanick J Crow; Koen Devriendt; Valérie Drouin-Garraud; Elisabeth Flori; David Geneviève; Raoul C Hennekam; Jane Hurst; Deborah Krakow; Martine Le Merrer; Klaske D Lichtenbelt; Sally A Lynch; Stanislas Lyonnet; Kay MacDermot; Sahar Mansour; André Megarbané; Heloisa G Santos; Miranda Splitt; Andrea Superti-Furga; Sheila Unger; Denise Williams; Arnold Munnich; Valérie Cormier-Daire
Journal:  J Med Genet       Date:  2011-03-17       Impact factor: 6.318

  3 in total

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