Literature DB >> 8513326

A missense mutation in type VII collagen in two affected siblings with recessive dystrophic epidermolysis bullosa.

A M Christiano1, D S Greenspan, G G Hoffman, X Zhang, Y Tamai, A N Lin, H C Dietz, A Hovnanian, J Uitto.   

Abstract

Recessive dystrophic epidermolysis bullosa is a severe mutilating genodermatosis. Previous ultrastructural demonstrations of altered anchoring fibrils, and recent genetic linkage analyses have suggested that type VII collagen, the major component of anchoring fibrils, is a candidate gene. We have identified a homozygous methionine-to-lysine mutation in two affected siblings, while their unaffected mother and half-brother are heterozygous carriers. The mutation resides in a highly conserved region of the C-terminus of type VII collagen, strongly suggesting that it is the cause of the disease in this family.

Entities:  

Mesh:

Substances:

Year:  1993        PMID: 8513326     DOI: 10.1038/ng0593-62

Source DB:  PubMed          Journal:  Nat Genet        ISSN: 1061-4036            Impact factor:   38.330


  40 in total

1.  Characterization of 18 new mutations in COL7A1 in recessive dystrophic epidermolysis bullosa provides evidence for distinct molecular mechanisms underlying defective anchoring fibril formation.

Authors:  A Hovnanian; A Rochat; C Bodemer; E Petit; C A Rivers; C Prost; S Fraitag; A M Christiano; J Uitto; M Lathrop; Y Barrandon; Y de Prost
Journal:  Am J Hum Genet       Date:  1997-09       Impact factor: 11.025

2.  COL7A1 mutation G2037E causes epidermal retention of type VII collagen.

Authors:  Daisuke Sawamura; Kazuko Sato-Matsumura; Satoko Shibata; Akari Tashiro; Masutaka Furue; Maki Goto; Kaori Sakai; Masashi Akiyama; Hideki Nakamura; Hiroshi Shimizu
Journal:  J Hum Genet       Date:  2006-03-24       Impact factor: 3.172

Review 3.  Epidermolysis bullosa: hereditary skin fragility diseases as paradigms in cell biology.

Authors:  R A Eady; M G Dunnill
Journal:  Arch Dermatol Res       Date:  1994       Impact factor: 3.017

4.  Compound heterozygosity for COL7A1 mutations in twins with dystrophic epidermolysis bullosa: a recessive paternal deletion/insertion mutation and a dominant negative maternal glycine substitution result in a severe phenotype.

Authors:  A M Christiano; I Anton-Lamprecht; S Amano; U Ebschner; R E Burgeson; J Uitto
Journal:  Am J Hum Genet       Date:  1996-04       Impact factor: 11.025

5.  Prenatal diagnosis for recessive dystrophic epidermolysis bullosa in 10 families by mutation and haplotype analysis in the type VII collagen gene (COL7A1).

Authors:  A M Christiano; S LaForgia; A S Paller; J McGuire; H Shimizu; J Uitto
Journal:  Mol Med       Date:  1996-01       Impact factor: 6.354

6.  Recurrent nonsense mutations within the type VII collagen gene in patients with severe recessive dystrophic epidermolysis bullosa.

Authors:  A Hovnanian; L Hilal; C Blanchet-Bardon; Y de Prost; A M Christiano; J Uitto; M Goossens
Journal:  Am J Hum Genet       Date:  1994-08       Impact factor: 11.025

7.  Expression of type VII collagen, the major anchoring fibril component, in normal and neoplastic human nervous system.

Authors:  W Paulus; I Baur; U Liszka; M Drlicek; I Leigh; L Bruckner-Tuderman
Journal:  Virchows Arch       Date:  1995       Impact factor: 4.064

8.  Dominant dystrophic epidermolysis bullosa: identification of a Gly-->Ser substitution in the triple-helical domain of type VII collagen.

Authors:  A M Christiano; M Ryynänen; J Uitto
Journal:  Proc Natl Acad Sci U S A       Date:  1994-04-26       Impact factor: 11.205

Review 9.  The molecular basis for inherited bullous diseases.

Authors:  B P Korge; T Krieg
Journal:  J Mol Med (Berl)       Date:  1996-02       Impact factor: 4.599

Review 10.  Oral manifestations in the epidermolysis bullosa spectrum.

Authors:  J Timothy Wright
Journal:  Dermatol Clin       Date:  2010-01       Impact factor: 3.478

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.