| Literature DB >> 8467839 |
L Chiadò-Piat1, T Mongini, C Doriguzzi, M Maniscalco, L Palmucci.
Abstract
Three cases of myophosphorylase deficiency with unusual clinical expression are presented. The 1st had clinical characteristics suggesting a mild congenital myopathy, and the patient never experienced cramps or myalgias. The 2nd had a slowly progressive myopathy without cramps or myoglobinuria which was detected by chance. The 3rd presented with myoglobinuria and acute renal failure, unrelated to a triggering effort, and with permanent weakness and wasting. In all cases, muscle biopsy demonstrated a vacuolar myopathy with free glycogen increase and absence of myophosphorylase activity, confirmed by biochemical assays. The cases confirm the wide clinical spectrum of McArdle disease.Entities:
Mesh:
Substances:
Year: 1993 PMID: 8467839 DOI: 10.1159/000116938
Source DB: PubMed Journal: Eur Neurol ISSN: 0014-3022 Impact factor: 1.710