Literature DB >> 8412008

Biochemical diagnosis of mucopolysaccharidoses: experience of 297 diagnoses in a 15-year period (1977-1991).

P Di Natale1, T Annella, A Daniele, T De Luca, E Morabito, R Pallini, P Rosario, G Spagnuolo.   

Abstract

We report the results over 15 years (1977-1991) for biochemical diagnoses of patients referred from throughout Italy and suspected of having a mucopolysaccharidosis. Of these, 147 patients were diagnosed as being homozygous or hemizygous for a specific lysosomal enzyme deficiency; 74 pregnancies at risk were monitored in their families; 76 heterozygote diagnoses were performed on their relatives, with a total of 48 positive diagnoses. We also report the analysis of genomic DNA from 11 unrelated Italian Hunter patients, using pc2S15 probe. DNA from two patients, digested with Pst-I, showed a variant pattern of hybridization caused by deletion or rearrangement of the gene.

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Year:  1993        PMID: 8412008     DOI: 10.1007/bf00710300

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  32 in total

1.  Gene diagnosis and carrier detection in Hunter syndrome by the iduronate-2-sulphatase cDNA probe.

Authors:  A Gal; M Beck; A C Sewell; C P Morris; E Schwinger; J J Hopwood
Journal:  J Inherit Metab Dis       Date:  1992       Impact factor: 4.982

2.  A fluorimetric enzyme assay for the diagnosis of Morquio disease type A (MPS IV A).

Authors:  O P van Diggelen; H Zhao; W J Kleijer; H C Janse; B J Poorthuis; J van Pelt; J P Kamerling; H Galjaard
Journal:  Clin Chim Acta       Date:  1990-02-28       Impact factor: 3.786

3.  Biochemical diagnosis of Hunter syndrome on Epstein-Barr virus-transformed lymphoblastoid cell lines.

Authors:  E Morabito; I Giambarrasi; M Rocchi; P Di Natale
Journal:  Clin Chim Acta       Date:  1989-05-15       Impact factor: 3.786

4.  The measurement of urinary mucopolysaccharides.

Authors:  N M Di Ferrante
Journal:  Anal Biochem       Date:  1967-10       Impact factor: 3.365

5.  Mucopolysaccharidosis VI (Maroteaux-Lamy syndrome). An intermediate clinical phenotype caused by substitution of valine for glycine at position 137 of arylsulfatase B.

Authors:  G Wicker; V Prill; D Brooks; G Gibson; J Hopwood; K von Figura; C Peters
Journal:  J Biol Chem       Date:  1991-11-15       Impact factor: 5.157

6.  Hunter syndrome: isolation of an iduronate-2-sulfatase cDNA clone and analysis of patient DNA.

Authors:  P J Wilson; C P Morris; D S Anson; T Occhiodoro; J Bielicki; P R Clements; J J Hopwood
Journal:  Proc Natl Acad Sci U S A       Date:  1990-11       Impact factor: 11.205

7.  A fluorometric assay using 4-methylumbelliferyl alpha-L-iduronide for the estimation of alpha-L-iduronidase activity and the detection of Hurler and Scheie syndromes.

Authors:  J J Hopwood; V Muller; A Smithson; N Baggett
Journal:  Clin Chim Acta       Date:  1979-03-01       Impact factor: 3.786

8.  A radioactive substrate and assay for alpha-L-iduronidase.

Authors:  P Di Natale; I G Leder; E F Neufeld
Journal:  Clin Chim Acta       Date:  1977-06-15       Impact factor: 3.786

9.  Prenatal diagnosis of mucopolysaccharidosis I: A special difficulty arising from an unusually low enzyme activity in mother's cells.

Authors:  R Gatti; C Borrone; M Filocamo; N Pannone; P Di Natale
Journal:  Prenat Diagn       Date:  1985 Mar-Apr       Impact factor: 3.050

10.  A direct spectrophotometric microassay for sulfated glycosaminoglycans in cartilage cultures.

Authors:  R W Farndale; C A Sayers; A J Barrett
Journal:  Connect Tissue Res       Date:  1982       Impact factor: 3.417

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  1 in total

1.  Heterogeneity of DNA and RNA in Hunter patients.

Authors:  T Annella; A Daniele; P Di Natale
Journal:  Hum Genet       Date:  1993-10       Impact factor: 4.132

  1 in total

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