Literature DB >> 8394635

Thiamine-responsive megaloblastic anemia with diabetes mellitus and sensorineural deafness.

A Akinci1, T Teziç, G Ertürk, O Tarim, K Dalva.   

Abstract

This study introduces a patient who has thiamine and thiamine pyrophosphokinase (TPKase) enzyme deficiency associated with diabetes mellitus, sensorineural deafness and thiamine-responsive megaloblastic anemia. Diabetes mellitus was diagnosed when she was 20 months old. After 1 year, macrocytic anemia developed and the thiamine therapy was started at 75 mg/day. During the follow-up, the insulin requirement decreased and even ceased, and macrocytic anemia improved with thiamine treatment. After thiamine therapy was ceased an increase in insulin requirement was observed and macrocytic anemia developed again.

Entities:  

Mesh:

Substances:

Year:  1993        PMID: 8394635     DOI: 10.1111/j.1442-200x.1993.tb03049.x

Source DB:  PubMed          Journal:  Acta Paediatr Jpn        ISSN: 0374-5600


  2 in total

1.  Localization of the gene for thiamine-responsive megaloblastic anemia syndrome, on the long arm of chromosome 1, by homozygosity mapping.

Authors:  E J Neufeld; H Mandel; T Raz; R Szargel; C N Yandava; A Stagg; S Fauré; T Barrett; N Buist; N Cohen
Journal:  Am J Hum Genet       Date:  1997-12       Impact factor: 11.025

2.  Thiamine-responsive megaloblastic anemia: identification of novel compound heterozygotes and mutation update.

Authors:  Anke K Bergmann; Inderneel Sahai; Jill F Falcone; Judy Fleming; Adam Bagg; Caterina Borgna-Pignati; Robin Casey; Luca Fabris; Elizabeth Hexner; Lulu Mathews; Maria Leticia Ribeiro; Klaas J Wierenga; Ellis J Neufeld
Journal:  J Pediatr       Date:  2009-07-29       Impact factor: 4.406

  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.