Literature DB >> 8037910

The ocular pathology in Leber's congenital amaurosis.

T J Sullivan1, J G Heathcote, S M Brazel, M A Musarella.   

Abstract

PURPOSE: To present the ocular pathology of a three-year-old child with Leber's congenital amaurosis (LCA) who died from an unrelated episode of presumed viral meningitis.
METHODS: Autopsy was performed, and in addition the globes were harvested for pathological examination. Before the child's death, known systemic disorders with infantile retinal dystrophy were excluded.
RESULTS: The outer nuclear layer and photoreceptor layers are the primary site of retinal pathology in LCA.
CONCLUSION: This report of the pathological findings in LCA, early in the natural history of the disease, indicates that process appears to be a degeneration rather than an agenesis.

Entities:  

Mesh:

Year:  1994        PMID: 8037910     DOI: 10.1111/j.1442-9071.1994.tb01691.x

Source DB:  PubMed          Journal:  Aust N Z J Ophthalmol        ISSN: 0814-9763


  2 in total

1.  An unusual retinal vascular morphology in connection with a novel AIPL1 mutation in Leber's congenital amaurosis.

Authors:  S Heegaard; T Rosenberg; M Preising; J U Prause; T Bek
Journal:  Br J Ophthalmol       Date:  2003-08       Impact factor: 4.638

2.  Identification of differentially regulated proteins in a patient with Leber's Congenital Amaurosis--a proteomic study.

Authors:  Henrik Vorum; Morten Østergaard; Greg E Rice; Bent Honoré; Toke Bek
Journal:  Proteome Sci       Date:  2007-02-27       Impact factor: 2.480

  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.