Literature DB >> 7726631

Molecular basis for the dystrophic forms of epidermolysis bullosa: mutations in the type VII collagen gene.

J Uitto1, A M Christiano.   

Abstract

Significant progress has recently been made in understanding the molecular basis of heritable skin diseases, such as epidermolysis bullosa, a group of mechano-bullous genodermatoses. In particular, the dystrophic forms of epidermolysis bullosa have been shown to result from distinct mutations in the gene encoding type VII collagen, the major, if not the exclusive, component of the anchoring fibrils. These mutations result in deficient synthesis and/or altered assembly of the anchoring fibrils, thus compromising the integrity of the cutaneous basement membrane zone. The mutations in the type VII collagen gene have implications for understanding the structure-function relationships of the type VII collagen molecule, and also provide the basis for prenatal DNA-based diagnosis in families at risk for recurrence of the disease. Finally, understanding the genetic basis of dystrophic forms of EB sets the stage for gene therapy approaches for the treatment of these devastating skin diseases.

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Year:  1994        PMID: 7726631     DOI: 10.1007/bf00370713

Source DB:  PubMed          Journal:  Arch Dermatol Res        ISSN: 0340-3696            Impact factor:   3.017


  35 in total

1.  Genetic linkage of type VII collagen (COL7A1) to dominant dystrophic epidermolysis bullosa in families with abnormal anchoring fibrils.

Authors:  M Ryynänen; J Ryynänen; S Sollberg; R V Iozzo; R G Knowlton; J Uitto
Journal:  J Clin Invest       Date:  1992-03       Impact factor: 14.808

2.  PCR-based detection of two exonic polymorphisms in the human type VII collagen gene (COL7A1) at 3p21.1.

Authors:  A M Christiano; L C Chung-Honet; A Hovnanian; J Uitto
Journal:  Genomics       Date:  1992-11       Impact factor: 5.736

Review 3.  Polymorphism of the human genome: markers for genetic linkage analyses in heritable diseases of the skin.

Authors:  A M Christiano; J Uitto
Journal:  J Invest Dermatol       Date:  1992-11       Impact factor: 8.551

4.  Type VII collagen gene expression by cultured human cells and in fetal skin. Abundant mRNA and protein levels in epidermal keratinocytes.

Authors:  J Ryynänen; S Sollberg; M G Parente; L C Chung; A M Christiano; J Uitto
Journal:  J Clin Invest       Date:  1992-01       Impact factor: 14.808

5.  The large non-collagenous domain (NC-1) of type VII collagen is amino-terminal and chimeric. Homology to cartilage matrix protein, the type III domains of fibronectin and the A domains of von Willebrand factor.

Authors:  A M Christiano; L M Rosenbaum; L C Chung-Honet; M G Parente; D T Woodley; T C Pan; R Z Zhang; M L Chu; R E Burgeson; J Uitto
Journal:  Hum Mol Genet       Date:  1992-10       Impact factor: 6.150

6.  Dominant dystrophic epidermolysis bullosa: identification of a Gly-->Ser substitution in the triple-helical domain of type VII collagen.

Authors:  A M Christiano; M Ryynänen; J Uitto
Journal:  Proc Natl Acad Sci U S A       Date:  1994-04-26       Impact factor: 11.205

7.  Linkage of autosomal dominant dystrophic epidermolysis bullosa in three British families to the marker D3S2 close to the COL7A1 locus.

Authors:  L al-Imara; A J Richards; R A Eady; I M Leigh; M Farrall; F M Pope
Journal:  J Med Genet       Date:  1992-06       Impact factor: 6.318

8.  Noncollagenous (NC1) domain of collagen VII resembles multidomain adhesion proteins involved in tissue-specific organization of extracellular matrix.

Authors:  W R Gammon; M L Abernethy; K M Padilla; P S Prisayanh; M E Cook; J Wright; R A Briggaman; S W Hunt
Journal:  J Invest Dermatol       Date:  1992-12       Impact factor: 8.551

9.  Human type VII collagen: cDNA cloning and chromosomal mapping of the gene.

Authors:  M G Parente; L C Chung; J Ryynänen; D T Woodley; K C Wynn; E A Bauer; M G Mattei; M L Chu; J Uitto
Journal:  Proc Natl Acad Sci U S A       Date:  1991-08-15       Impact factor: 11.205

Review 10.  DNA-based prenatal diagnosis of heritable skin diseases.

Authors:  A M Christiano; J Uitto
Journal:  Arch Dermatol       Date:  1993-11
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  18 in total

1.  Characterization of 18 new mutations in COL7A1 in recessive dystrophic epidermolysis bullosa provides evidence for distinct molecular mechanisms underlying defective anchoring fibril formation.

Authors:  A Hovnanian; A Rochat; C Bodemer; E Petit; C A Rivers; C Prost; S Fraitag; A M Christiano; J Uitto; M Lathrop; Y Barrandon; Y de Prost
Journal:  Am J Hum Genet       Date:  1997-09       Impact factor: 11.025

2.  Aminoglycosides restore full-length type VII collagen by overcoming premature termination codons: therapeutic implications for dystrophic epidermolysis bullosa.

Authors:  Jon Cogan; Jacqueline Weinstein; Xinyi Wang; Yingping Hou; Sabrina Martin; Andrew P South; David T Woodley; Mei Chen
Journal:  Mol Ther       Date:  2014-07-23       Impact factor: 11.454

3.  Superficial dermal fibroblasts enhance basement membrane and epidermal barrier formation in tissue-engineered skin: implications for treatment of skin basement membrane disorders.

Authors:  Mathew Varkey; Jie Ding; Edward E Tredget
Journal:  Tissue Eng Part A       Date:  2013-10-17       Impact factor: 3.845

4.  Epidermolysis bullosa with pyloric atresia: novel mutations in the beta4 integrin gene (ITGB4).

Authors:  L Pulkkinen; D U Kim; J Uitto
Journal:  Am J Pathol       Date:  1998-01       Impact factor: 4.307

5.  Prenatal diagnosis for recessive dystrophic epidermolysis bullosa in 10 families by mutation and haplotype analysis in the type VII collagen gene (COL7A1).

Authors:  A M Christiano; S LaForgia; A S Paller; J McGuire; H Shimizu; J Uitto
Journal:  Mol Med       Date:  1996-01       Impact factor: 6.354

6.  Gentamicin induces functional type VII collagen in recessive dystrophic epidermolysis bullosa patients.

Authors:  David T Woodley; Jon Cogan; Yingping Hou; Chao Lyu; M Peter Marinkovich; Douglas Keene; Mei Chen
Journal:  J Clin Invest       Date:  2017-07-10       Impact factor: 14.808

7.  Characterization of molecular mechanisms underlying mutations in dystrophic epidermolysis bullosa using site-directed mutagenesis.

Authors:  David T Woodley; Yingping Hou; Sabrina Martin; Wei Li; Mei Chen
Journal:  J Biol Chem       Date:  2008-04-30       Impact factor: 5.157

8.  Glycine substitutions in the triple-helical region of type VII collagen result in a spectrum of dystrophic epidermolysis bullosa phenotypes and patterns of inheritance.

Authors:  A M Christiano; J A McGrath; K C Tan; J Uitto
Journal:  Am J Hum Genet       Date:  1996-04       Impact factor: 11.025

Review 9.  Type VII collagen: the anchoring fibril protein at fault in dystrophic epidermolysis bullosa.

Authors:  Hye Jin Chung; Jouni Uitto
Journal:  Dermatol Clin       Date:  2010-01       Impact factor: 3.478

10.  Topical application of recombinant type VII collagen incorporates into the dermal-epidermal junction and promotes wound closure.

Authors:  Xinyi Wang; Pedram Ghasri; Mahsa Amir; Brian Hwang; Yingpin Hou; Michael Khalili; Michael Khilili; Andrew Lin; Douglas Keene; Jouni Uitto; David T Woodley; Mei Chen
Journal:  Mol Ther       Date:  2013-05-14       Impact factor: 11.454

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