Literature DB >> 7710377

Clinical symptoms of adult metachromatic leukodystrophy and arylsulfatase A pseudodeficiency.

A T Hageman1, F J Gabreëls, J G de Jong, A A Gabreëls-Festen, C J van den Berg, B A van Oost, R A Wevers.   

Abstract

OBJECTIVE: To determine the clinical symptoms in adult metachromatic leukodystrophy and in adult pseudodeficiency for arylsulfatase A.
DESIGN: Case series.
SETTING: University hospital. PATIENTS: Twenty-five adult patients with very low arylsulfatase A activity.
RESULTS: In 13 patients, a diagnosis of adult metachromatic leukodystrophy was made. The main symptoms were dementia, behavioral abnormalities, ataxia, and polyneuropathy. In 12 patients, a diagnosis of arylsulfatase A pseudodeficiency was made. No characteristic clinical syndrome could be detected in these patients.
CONCLUSIONS: Adult metachromatic leukodystrophy is a progressive metabolic disease with symptoms of demyelination of the central and peripheral nervous systems. Diagnosis must be confirmed by determination of arylsulfatase A activity and accumulation of sulfatides. Pseudodeficiency for arylsulfatase A can be confirmed or excluded by means of DNA analysis.

Entities:  

Mesh:

Substances:

Year:  1995        PMID: 7710377     DOI: 10.1001/archneur.1995.00540280098023

Source DB:  PubMed          Journal:  Arch Neurol        ISSN: 0003-9942


  8 in total

1.  Hematopoietic SCT: a useful treatment for late metachromatic leukodystrophy.

Authors:  M Solders; D A Martin; C Andersson; M Remberger; T Andersson; O Ringdén; G Solders
Journal:  Bone Marrow Transplant       Date:  2014-05-05       Impact factor: 5.483

2.  Adult metachromatic leukodystrophy: disorganized schizophrenia-like symptoms and postpartum depression in 2 sisters.

Authors:  Hojka Gregoric Kumperscak; Eduard Paschke; Peter Gradisnik; Jernej Vidmar; Stanislava Umek Bradac
Journal:  J Psychiatry Neurosci       Date:  2005-01       Impact factor: 6.186

3.  Rare Diseases in Glycosphingolipid Metabolism.

Authors:  Hongwen Zhou; Zhoulu Wu; Yiwen Wang; Qinyi Wu; Moran Hu; Shuai Ma; Min Zhou; Yan Sun; Baowen Yu; Jingya Ye; Wanzi Jiang; Zhenzhen Fu; Yingyun Gong
Journal:  Adv Exp Med Biol       Date:  2022       Impact factor: 2.622

4.  Brain Reserve in a Case of Cognitive Resilience to Severe Leukoaraiosis.

Authors:  Dana M Szeles; Nicholas J Milano; Hunter J Moss; Maria Vittoria Spampinato; Jens H Jensen; Andreana Benitez
Journal:  J Int Neuropsychol Soc       Date:  2020-06-16       Impact factor: 2.892

Review 5.  Peripheral neuropathy in metachromatic leukodystrophy: current status and future perspective.

Authors:  Shanice Beerepoot; Stefan Nierkens; Jaap Jan Boelens; Caroline Lindemans; Marianna Bugiani; Nicole I Wolf
Journal:  Orphanet J Rare Dis       Date:  2019-11-04       Impact factor: 4.123

6.  Case Report: Novel Arylsulfatase A (ARSA) Gene Mutations in a Patient With Adult-Onset Metachromatic Leukodystrophy Misdiagnosed as Multiple Sclerosis.

Authors:  Lulu Xu; Meixiang Zhong; Yajuan Wang; Zhihong Wang; Jie Song; Jing Zhao; Hongyun Yu; Zhencui Yang; Wenjing Yan; Xueping Zheng
Journal:  Front Neurol       Date:  2021-01-11       Impact factor: 4.003

7.  Volumetric MRI data correlate to disease severity in metachromatic leukodystrophy.

Authors:  Jan-Mendelt Tillema; Marloes Gm Derks; Petra J W Pouwels; Pim de Graaf; Diane F van Rappard; Frederik Barkhof; Marjan E Steenweg; Marjo S van der Knaap; Nicole I Wolf
Journal:  Ann Clin Transl Neurol       Date:  2015-08-24       Impact factor: 4.511

8.  Adult onset subacute sclerosing panencephalitis - Lessons learnt from an atypical presentation.

Authors:  Mahendra Javali; Ramshekar Menon; Rahul Chakor
Journal:  J Neurosci Rural Pract       Date:  2014-07
  8 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.