Literature DB >> 7009026

Subcellular fractionation studies on hepatic tissue from a patient with Pompe's disease (type II glycogen-storage disease).

T J Peters, W Jenkins, V Dubowitz.   

Abstract

1. An homogenate of liver biopsy taken from a patient with Pompe's disease (type II glycogen-storage disease) was analysed by enzyme microassay and subcellular fractionation by sucrose-density-gradient centrifugation. 2. A strikingly low activity of lysosomal acid alpha-D-glucosidase was noted but there was also increased activity of neutral alpha-D-glucosidase (found in endoplasmic reticulum). 3. Activities of the acid hydrolases, acid phosphatase and beta-N-acetyl-D-glucosaminidase, were elevated compared with those of controls. Measurement of latent beta-N-acetyl-D-glucosaminidase activity and results of subcellular fractionation experiments, indicated a marked fragility of certain populations of lysosomes. Lysosomes containing predominantly acid phosphatase and beta-D-glucuronidase activities appeared to have normal integrity. 4. Assessment of organelle pathology by enzyme microassay indicated low mitochondrial and peroxisomal enzyme activities. In addition there was evidence of mitochondrial damage as reflected by increased sucrose permeability and by ultrastructural studies.

Entities:  

Mesh:

Substances:

Year:  1980        PMID: 7009026     DOI: 10.1042/cs0590007

Source DB:  PubMed          Journal:  Clin Sci (Lond)        ISSN: 0143-5221            Impact factor:   6.124


  5 in total

1.  The incorporation in vitro of sulphate ions into synaptic-membrane glycoproteins.

Authors:  C J White
Journal:  Biochem J       Date:  1981-11-15       Impact factor: 3.857

2.  Juvenile acid maltase deficiency presenting as paravertebral pseudotumour.

Authors:  T C Iancu; A Lerner; H Shiloh; N Bashan; S Moses
Journal:  Eur J Pediatr       Date:  1988-05       Impact factor: 3.183

3.  Comparative pathology of the canine model of glycogen storage disease type II (Pompe's disease).

Authors:  H C Walvoort; J A Dormans; T S van den Ingh
Journal:  J Inherit Metab Dis       Date:  1985       Impact factor: 4.982

4.  Investigation of tissue organelles by a combination of analytical subcellular fractionation and enzymic microanalysis: a new approach to pathology.

Authors:  T J Peters
Journal:  J Clin Pathol       Date:  1981-01       Impact factor: 3.411

5.  Castanospermine inhibits alpha-glucosidase activities and alters glycogen distribution in animals.

Authors:  R Saul; J J Ghidoni; R J Molyneux; A D Elbein
Journal:  Proc Natl Acad Sci U S A       Date:  1985-01       Impact factor: 11.205

  5 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.