Literature DB >> 6982283

Aberrant multimeric structure of von Willebrand factor in a new variant of von Willebrand's disease (type IIC).

Z M Ruggeri, I M Nilsson, R Lombardi, L Holmberg, T S Zimmerman.   

Abstract

A variant of von Willebrand's disease has been identified in which sodium dodecyl sulfate agarose electrophoresis provides evidence that the von Willebrand factor present is structurally abnormal. Rather than the repeating triplet seen in normal subjects and in patients with the IIA and IIB variants, a repeating doublet was present in the propositus. None of the bands had the same mobility as bands in normal subjects or previously described von Willebrand's disease patients. The larger multimers of von Willebrand factor were lacking both from plasma and platelets, and did not appear in the circulation after infusion of 1-deamino-[8-D-arginine]-vasopressin. There was a marked increase in the concentration of the smallest multimer in the propositus and his phenotypically normal children, indicating that this abnormality of von Willebrand factor is inherited in an autosomal-recessive manner.

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Year:  1982        PMID: 6982283      PMCID: PMC370325          DOI: 10.1172/jci110700

Source DB:  PubMed          Journal:  J Clin Invest        ISSN: 0021-9738            Impact factor:   14.808


  8 in total

1.  Two populations of factor VIII-related antigen in a family with von Willebrand's disease.

Authors:  H Armitage; C R Rizza
Journal:  Br J Haematol       Date:  1979-02       Impact factor: 6.998

2.  Structural analysis of factor VIII antigen in von Willebrand disease.

Authors:  R L Nachman; E A Jaffe; C Miller; W T Brown
Journal:  Proc Natl Acad Sci U S A       Date:  1980-11       Impact factor: 11.205

3.  Disulfide bonds and the quaternary structure of factor VIII/von Willebrand factor.

Authors:  R B Counts; S L Paskell; S K Elgee
Journal:  J Clin Invest       Date:  1978-09       Impact factor: 14.808

4.  Variant von Willebrand's disease: characterization of two subtypes by analysis of multimeric composition of factor VIII/von Willebrand factor in plasma and platelets.

Authors:  Z M Ruggeri; T S Zimmerman
Journal:  J Clin Invest       Date:  1980-06       Impact factor: 14.808

5.  Multimeric composition of factor VIII/von Willebrand factor following administration of DDAVP: implications for pathophysiology and therapy of von Willebrand's disease subtypes.

Authors:  Z M Ruggeri; P M Mannucci; R Lombardi; A B Federici; T S Zimmerman
Journal:  Blood       Date:  1982-06       Impact factor: 22.113

6.  Heightened interaction between platelets and factor VIII/von Willebrand factor in a new subtype of von Willebrand's disease.

Authors:  Z M Ruggeri; F I Pareti; P M Mannucci; N Ciavarella; T S Zimmerman
Journal:  N Engl J Med       Date:  1980-05-08       Impact factor: 91.245

7.  Factor VIII-related protein circulates in normal human plasma as high molecular weight multimers.

Authors:  L W Hoyer; J R Shainoff
Journal:  Blood       Date:  1980-06       Impact factor: 22.113

8.  The complex multimeric composition of factor VIII/von Willebrand factor.

Authors:  Z M Ruggeri; T S Zimmerman
Journal:  Blood       Date:  1981-06       Impact factor: 22.113

  8 in total
  16 in total

1.  The mutation N528S in the von Willebrand factor (VWF) propeptide causes defective multimerization and storage of VWF.

Authors:  Sandra L Haberichter; Ulrich Budde; Tobias Obser; Sonja Schneppenheim; Cornelia Wermes; Reinhard Schneppenheim
Journal:  Blood       Date:  2010-03-24       Impact factor: 22.113

2.  Cloning and characterization of two cDNAs coding for human von Willebrand factor.

Authors:  J E Sadler; B B Shelton-Inloes; J M Sorace; J M Harlan; K Titani; E W Davie
Journal:  Proc Natl Acad Sci U S A       Date:  1985-10       Impact factor: 11.205

3.  Defective dimerization of von Willebrand factor subunits due to a Cys-> Arg mutation in type IID von Willebrand disease.

Authors:  R Schneppenheim; J Brassard; S Krey; U Budde; T J Kunicki; L Holmberg; J Ware; Z M Ruggeri
Journal:  Proc Natl Acad Sci U S A       Date:  1996-04-16       Impact factor: 11.205

Review 4.  Von Willebrand's disease.

Authors:  I M Nilsson; S Lethagen
Journal:  Indian J Pediatr       Date:  1993 Mar-Apr       Impact factor: 1.967

5.  Simultaneous inheritance and expression of classical haemophilia A and type IIA von Willebrand's disease.

Authors:  A C Beddall; S M Enayat; C E Williams; P E Short; F G Hill
Journal:  J Clin Pathol       Date:  1984-09       Impact factor: 3.411

6.  Carbohydrate moiety of von Willebrand factor is not necessary for maintaining multimeric structure and ristocetin cofactor activity but protects from proteolytic degradation.

Authors:  A B Federici; J H Elder; L De Marco; Z M Ruggeri; T S Zimmerman
Journal:  J Clin Invest       Date:  1984-12       Impact factor: 14.808

7.  Identification and characterization of the elusive mutation causing the historical von Willebrand Disease type IIC Miami.

Authors:  T Obser; M Ledford-Kraemer; F Oyen; M A Brehm; C V Denis; R Marschalek; R R Montgomery; J E Sadler; S Schneppenheim; U Budde; R Schneppenheim
Journal:  J Thromb Haemost       Date:  2016-08-20       Impact factor: 5.824

8.  Heterogeneity of plasma von Willebrand factor multimers resulting from proteolysis of the constituent subunit.

Authors:  J A Dent; M Galbusera; Z M Ruggeri
Journal:  J Clin Invest       Date:  1991-09       Impact factor: 14.808

9.  Triplet structure of von Willebrand factor reflects proteolytic degradation of high molecular weight multimers.

Authors:  M Furlan; R Robles; D Affolter; D Meyer; P Baillod; B Lämmle
Journal:  Proc Natl Acad Sci U S A       Date:  1993-08-15       Impact factor: 11.205

10.  Investigation of a kindred with a new autosomal dominantly inherited variant type von Willebrand's disease (possible type IID).

Authors:  F G Hill; M S Enayat; A J George
Journal:  J Clin Pathol       Date:  1985-06       Impact factor: 3.411

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