Literature DB >> 6842197

Neurological features and computed tomography of the brain in children with ornithine carbamoyl transferase deficiency.

B E Kendall, D P Kingsley, J V Leonard, S Lingam, V G Oberholzer.   

Abstract

The clinical features and the computed tomographic appearances of the brain in seven children with ornithine carbamoyl transferase deficiency are described. Episodic vomiting and drowsiness, acute encephalopathy, failure to thrive and developmental retardation were common, but focal neurological symptoms and signs were also observed. The CT appearances were non-specific with generalised or focal changes. They were related to the severity, the duration and the age of onset of the hyperammonaemia. Since the CT changes may suggest conditions other than metabolic disease, the emergency investigation of a child with an encephalopathy should include the estimation of plasma ammonium and, if elevated, the appropriate investigations to establish the cause.

Entities:  

Mesh:

Substances:

Year:  1983        PMID: 6842197      PMCID: PMC1027260          DOI: 10.1136/jnnp.46.1.28

Source DB:  PubMed          Journal:  J Neurol Neurosurg Psychiatry        ISSN: 0022-3050            Impact factor:   10.154


  19 in total

1.  Hereditary ornithine transcarbamylase deficiency. Report of two male cases with residual enzymatic activity.

Authors:  J M Saudubray; L Cathelineau; J M Laugier; C Charpentier; J A Lejeune; P Mozziconacci
Journal:  Acta Paediatr Scand       Date:  1975-05

2.  [Hereditary ornithine-carbamyl-transferase deficiency with qualitative enzyme abnormality. Report of a form with neonatal revelation and fatal course in a boy].

Authors:  J M Saudubray; L Cathelineau; C Charpentier; J Boisse; C Allaneau; H Le Bont; B Lesage
Journal:  Arch Fr Pediatr       Date:  1973-01

3.  Evidence for x-linked dominant inheritance of ornithine transcarbamylase deficiency.

Authors:  E M Short; H O Conn; P J Snodgrass; A G Campbell; L E Rosenberg
Journal:  N Engl J Med       Date:  1973-01-04       Impact factor: 91.245

4.  Hyperammonemia due to a defect in hepatic ornithine transcarbamylase.

Authors:  P Sunshine; J E Lindenbaum; H L Levy; J M Freeman
Journal:  Pediatrics       Date:  1972-07       Impact factor: 7.124

5.  Hyperammonaemia. A variant type of deficiency of liver ornithine transcarbamylase.

Authors:  B Levin; R H Dobbs; E A Burgess; T Palmer
Journal:  Arch Dis Child       Date:  1969-04       Impact factor: 3.791

6.  beta-Hydroxy-beta-methyglutaricaciduria presenting as Reye's syndrome.

Authors:  J V Leonard; J W Seakins; N K Griffin
Journal:  Lancet       Date:  1979-03-24       Impact factor: 79.321

7.  Demyelinating and neuro-degenerative disease in childhood. CT appearances and their differential diagnosis.

Authors:  D P Kingsley; B E Kendall
Journal:  J Neuroradiol       Date:  1981       Impact factor: 3.447

8.  Comparison of exchange transfusion, peritoneal dialysis, and hemodialysis for the treatment of hyperammonemia in an anuric newborn infant.

Authors:  S M Donn; R D Swartz; J G Thoene
Journal:  J Pediatr       Date:  1979-07       Impact factor: 4.406

9.  Systemic carnitine deficiency. Report of a fatal case with multisystemic manifestations.

Authors:  A J Ware; W C Burton; J D McGarry; J F Marks; A G Weinberg
Journal:  J Pediatr       Date:  1978-12       Impact factor: 4.406

10.  Atypical clinical course of ornithine transcarbamylase deficiency due to a new mutant (comparison with Reye's disease).

Authors:  I Krieger; P J Snodgrass; J Roskamp
Journal:  J Clin Endocrinol Metab       Date:  1979-03       Impact factor: 5.958

View more
  10 in total

1.  Neurological outcome of patients with ornithine carbamoyltransferase deficiency.

Authors:  P Nicolaides; D Liebsch; N Dale; J Leonard; R Surtees
Journal:  Arch Dis Child       Date:  2002-01       Impact factor: 3.791

Review 2.  Pathogenesis of hepatic encephalopathy: role of ammonia and systemic inflammation.

Authors:  Dominic R Aldridge; Edward J Tranah; Debbie L Shawcross
Journal:  J Clin Exp Hepatol       Date:  2014-06-30

3.  The early detection and management of inborn errors presenting acutely in the neonatal period.

Authors:  J V Leonard
Journal:  Eur J Pediatr       Date:  1985-03       Impact factor: 3.183

Review 4.  Acute metabolic encephalopathy: a review of causes, mechanisms and treatment.

Authors:  R Surtees; J V Leonard
Journal:  J Inherit Metab Dis       Date:  1989       Impact factor: 4.982

Review 5.  Pathophysiology of hepatic encephalopathy: a new look at ammonia.

Authors:  Roger F Butterworth
Journal:  Metab Brain Dis       Date:  2002-12       Impact factor: 3.584

Review 6.  Tools for diagnosis of leukodystrophies and other disorders presenting with white matter disease.

Authors:  Adeline Vanderver
Journal:  Curr Neurol Neurosci Rep       Date:  2005-03       Impact factor: 5.081

Review 7.  Effects of hyperammonaemia on brain function.

Authors:  R F Butterworth
Journal:  J Inherit Metab Dis       Date:  1998       Impact factor: 4.982

8.  Ornithine carbamoyl transferase deficiency: a neuropathological study.

Authors:  B N Harding; J V Leonard; M Erdohazi
Journal:  Eur J Pediatr       Date:  1984-02       Impact factor: 3.183

9.  Late onset ornithine carbamoyl transferase deficiency in males.

Authors:  E Drogari; J V Leonard
Journal:  Arch Dis Child       Date:  1988-11       Impact factor: 3.791

10.  Urea cycle defect: a case with MR and CT findings resembling infarct.

Authors:  A C Mamourian; A du Plessis
Journal:  Pediatr Radiol       Date:  1991
  10 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.