Literature DB >> 6747661

Behr's syndrome. A family exhibiting pseudodominant inheritance.

P K Thomas, J M Workman, O Thage.   

Abstract

A family with the clinical features of Behr's syndrome is described that exhibited probable pseudodominant inheritance. The salient clinical manifestations consisted of mental retardation and dementia, optic atrophy, cerebellar ataxia, pyramidal signs and peripheral neuropathy. Nerve biopsy from the index case showed a chronic neuropathy with axonal degeneration and regeneration. A muscle biopsy from the same patient demonstrated multiple inclusions composed of spiral cylindrical structures possibly derived from the sarcoplasmic reticulum, and less obtrusive accumulations of mitochondria, some of which contained paracrystalline inclusions.

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Year:  1984        PMID: 6747661     DOI: 10.1016/0022-510x(84)90032-7

Source DB:  PubMed          Journal:  J Neurol Sci        ISSN: 0022-510X            Impact factor:   3.181


  4 in total

1.  High serum creatine kinase levels associated with cylindrical spirals at muscle biopsy.

Authors:  S Rapuzzi; A Prelle; M Moggio; C Rigoletto; P Ciscato; G Comi; F Francesca; G Scarlato
Journal:  Acta Neuropathol       Date:  1995       Impact factor: 17.088

2.  Peroneal muscular atrophy with hereditary spastic paraparesis (HMSN V) is pathologically heterogeneous. Report of nerve biopsy in four cases and review of the literature.

Authors:  F Gemignani; D Guidetti; P Bizzi; P Preda; G Cenacchi; A Marbini
Journal:  Acta Neuropathol       Date:  1992       Impact factor: 17.088

Review 3.  Recessive optic atrophy, sensorimotor neuropathy and cataract associated with novel compound heterozygous mutations in OPA1.

Authors:  Jinho Lee; Sung-Chul Jung; Young Bin Hong; Jeong Hyun Yoo; Heasoo Koo; Ja Hyun Lee; Hyun Dae Hong; Sang-Beom Kim; Ki Wha Chung; Byung-Ok Choi
Journal:  Mol Med Rep       Date:  2016-05-04       Impact factor: 2.952

4.  Behr's Syndrome is Typically Associated with Disturbed Mitochondrial Translation and Mutations in the C12orf65 Gene.

Authors:  Angela Pyle; Venkateswaran Ramesh; Marina Bartsakoulia; Veronika Boczonadi; Aurora Gomez-Duran; Agnes Herczegfalvi; Emma L Blakely; Tania Smertenko; Jennifer Duff; Gail Eglon; David Moore; Patrick Yu-Wai-Man; Konstantinos Douroudis; Mauro Santibanez-Koref; Helen Griffin; Hanns Lochmüller; Veronika Karcagi; Robert W Taylor; Patrick F Chinnery; Rita Horvath
Journal:  J Neuromuscul Dis       Date:  2014
  4 in total

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