Literature DB >> 6591877

Clinical varieties of neuromuscular disease in debrancher deficiency.

F Cornelio, N Bresolin, P A Singer, S DiMauro, L P Rowland.   

Abstract

Two men and one woman with debrancher deficiency had symptoms and signs of neuromuscular disease. The two men had adult-onset and slowly progressive weakness, distal muscle wasting, "mixed" electromyographic patterns, and slow nerve conduction velocities; the initial diagnosis was Charcot-Marie-Tooth disease in one patient and motor neuron disease in the other. The woman had stunted growth, delayed motor milestones, and lifelong nonprogressive weakness. A muscle biopsy specimen showed severe vacuolar myopathy in all three cases. The glycogen concentration was increased threefold to sixfold and had an abnormal iodine spectrum. Anaerobic glycolysis in vitro showed impaired use of endogenous and exogenous glycogen but normal use of hexose-phosphate glycolytic intermediates. These three cases illustrated the clinical variety of neuromuscular disease in debrancher deficiency. In patients with weakness of adult onset, the diagnosis is impossible to make without performing a muscle biopsy.

Entities:  

Mesh:

Year:  1984        PMID: 6591877     DOI: 10.1001/archneur.1984.04050210025008

Source DB:  PubMed          Journal:  Arch Neurol        ISSN: 0003-9942


  7 in total

Review 1.  Myopathies Related to Glycogen Metabolism Disorders.

Authors:  Mark A Tarnopolsky
Journal:  Neurotherapeutics       Date:  2018-10       Impact factor: 7.620

2.  [Polyglycosan body myopathy].

Authors:  M Jeub; K Kappes-Horn; C Kornblum; D Fischer
Journal:  Nervenarzt       Date:  2006-12       Impact factor: 1.214

3.  Different clinical aspects of debrancher deficiency myopathy.

Authors:  S Kiechl; U Kohlendorfer; C Thaler; D Skladal; M Jaksch; B Obermaier-Kusser; J Willeit
Journal:  J Neurol Neurosurg Psychiatry       Date:  1999-09       Impact factor: 10.154

4.  Debrancher deficiency neuromuscular disorder with pseudohypertrophy in two brothers.

Authors:  A Marbini; F Gemignani; F Saccardi; M Rimoldi
Journal:  J Neurol       Date:  1989-10       Impact factor: 4.849

5.  Myopathies due to enzyme deficiencies.

Authors:  F Cornelio; S Di Donato
Journal:  J Neurol       Date:  1985       Impact factor: 4.849

Review 6.  Differential diagnosis of idiopathic inflammatory myopathies.

Authors:  Alan N Baer
Journal:  Curr Rheumatol Rep       Date:  2006-06       Impact factor: 4.686

7.  Comparison of gluteus medius muscle activity in Haflinger and Noriker horses with polysaccharide storage myopathy.

Authors:  Rebeka Roza Zsoldos; Negar Khayatzadeh; Johann Soelkner; Ulrike Schroeder; Caroline Hahn; Theresia Franziska Licka
Journal:  J Anim Physiol Anim Nutr (Berl)       Date:  2021-02-20       Impact factor: 2.718

  7 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.