Literature DB >> 6452514

Needle muscle biopsy for carrier detection in Duchenne muscular dystrophy. Part 1. Light microscopy--histology, histochemistry and quantitation.

C A Maunder-Sewry, V Dubowitz.   

Abstract

Needle muscle biopsies from 14 genetically proven carriers of Duchenne muscular dystrophy (DMD), 14 possible carriers with elevated serum creatine kinase activity (SCK) and 37 possible carriers with normal SCK were compared with similar samples from 10 healthy volunteer females with the aim of identifying subtle changes that might aid carrier detection. Qualitative differences were similar to those previously reported and included variation in fibre size, an increase in the number of internal nuclei and fragmentation of the myofibrillar network. By visual assessment, only 11% of the biopsies were classified as unequivocally abnormal but quantitation of fibre type proportions, fibre diameters and the number of internal nuclei showed that 71% of definite carriers, 86% of possible carriers with elevated SCK and 78% of possible carriers with normal SCK had at least one feature that was significantly different from controls. The commonest abnormalities were an increase in the proportion of type 1 fibres, an alteration in the mean diameter ratio of type 1:type 2 fibres, an increase in the fibre diameter variation coefficient and an increase in the number of internal nuclei. The changes in definite carriers were not related to elevated SCK and several with normal SCK showed morphological differences. It was concluded that quantitation of morphological features is essential for a full appraisal of biopsies from DMD carriers and that this approach is a useful aid to carrier detection.

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Year:  1981        PMID: 6452514     DOI: 10.1016/0022-510x(81)90087-3

Source DB:  PubMed          Journal:  J Neurol Sci        ISSN: 0022-510X            Impact factor:   3.181


  6 in total

1.  Needle biopsy for muscle diagnosis and research: an Italian experience.

Authors:  F Dworzak; L Morandi; S Daniel; I Dones; F Blasevich; M Marchi; M Mora; M Rimoldi; F Cornelio
Journal:  Ital J Neurol Sci       Date:  1987-08

Review 2.  Duchenne muscular dystrophy: pathogenetic aspects and genetic prevention.

Authors:  H Moser
Journal:  Hum Genet       Date:  1984       Impact factor: 4.132

3.  Diagnostic needle muscle biopsy. A practical and reliable alternative to open biopsy.

Authors:  J Z Heckmatt; A Moosa; C Hutson; C A Maunder-Sewry; V Dubowitz
Journal:  Arch Dis Child       Date:  1984-06       Impact factor: 3.791

4.  The female carrier of Duchenne muscular dystrophy.

Authors:  V Dubowitz
Journal:  Br Med J (Clin Res Ed)       Date:  1982-05-15

5.  Genetics of congenital nemaline myopathy: a study of 10 families.

Authors:  C Wallgren-Pettersson; H Kääriäinen; J Rapola; T Salmi; J Jääskeläinen; M Donner
Journal:  J Med Genet       Date:  1990-08       Impact factor: 6.318

6.  A cell surface abnormality in Duchenne muscular dystrophy: intercellular adhesiveness of skin fibroblasts from patients and carriers.

Authors:  G E Jones; J A Witkowski
Journal:  Hum Genet       Date:  1983       Impact factor: 4.132

  6 in total

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