Literature DB >> 6375356

Enzymatic and immunological studies of uroporphyrinogen decarboxylase in familial porphyria cutanea tarda and hepatoerythropoietic porphyria.

H de Verneuil, C Beaumont, J C Deybach, Y Nordmann, Z Sfar, R Kastally.   

Abstract

Uroporphyrinogen decarboxylase activity was measured in hemoglobin-free lysates from two patients with hepatoerythropoietic porphyria (HEP) and from 12 unrelated patients with familial porphyria cutanea tarda (PCT). In HEP patients, enzyme activities were 5% of normal, and familial studies clearly confirmed that patients with HEP are cases of homozygous PCT. Immunoreactive uroporphyrinogen decarboxylase was measured by developing a direct and noncompetitive enzyme immunoassay (EIA). For the 12 familial PCT patients, we found an immunoreactive protein decreased (51%) to the same extent as the catalytic activity (48%) [cross-reactive immunological material ( CRIM ) negative]. The children from the HEP family were also CRIM negative, contrasting with another HEP family previously described as CRIM positive; our data support the hypothesis of a heterogeneity in familial uroporphyrinogen decarboxylase deficiency.

Entities:  

Mesh:

Substances:

Year:  1984        PMID: 6375356      PMCID: PMC1684444     

Source DB:  PubMed          Journal:  Am J Hum Genet        ISSN: 0002-9297            Impact factor:   11.025


  22 in total

1.  Immunochemical studies on electron transport chains involving cytochrome P-450. I. Effects of antibodies to pig liver microsomal reduced triphosphopyridine nucleotide-cytochrome c reductase and the non-heme iron protein from bovine adrenocortical mitochondria.

Authors:  B S Masters; J Baron; W E Taylor; E L Isaacson; J LoSpalluto
Journal:  J Biol Chem       Date:  1971-07-10       Impact factor: 5.157

2.  Porphyrin distribution and porphyrin excretion in human congenital erythropoietic porphyria.

Authors:  L Eriksen; N Eriksen
Journal:  Scand J Clin Lab Invest       Date:  1974-06       Impact factor: 1.713

3.  Peroxidase labelled antibody and Fab conjugates with enhanced intracellular penetration.

Authors:  S Avrameas; T Ternynck
Journal:  Immunochemistry       Date:  1971-12

4.  The pattern of porphyrin isomer accumulation and excretion in symptomatic porphyria.

Authors:  E Dowdle; P Goldswain; N Spong; L Eales
Journal:  Clin Sci       Date:  1970-08       Impact factor: 6.124

5.  A case of biochemically unclassifiable hepatic porphyria.

Authors:  J P Aguadé; A Castells; A Indacochea; J Rodés
Journal:  Br J Dermatol       Date:  1969-04       Impact factor: 9.302

6.  Cosmetic talc powder.

Authors: 
Journal:  Lancet       Date:  1977-06-25       Impact factor: 79.321

7.  Familial and sporadic porphyria cutanea: two different diseases.

Authors:  H de Verneuil; G Aitken; Y Nordmann
Journal:  Hum Genet       Date:  1978-10-31       Impact factor: 4.132

8.  Decreased activity of hepatic uroporphyrinogen decarboxylase in sporadic porphyria cutanea tarda.

Authors:  G H Elder; G B Lee; J A Tovey
Journal:  N Engl J Med       Date:  1978-08-10       Impact factor: 91.245

9.  An inherited enzymatic defect in porphyria cutanea tarda: decreased uroporphyrinogen decarboxylase activity.

Authors:  J P Kushner; A J Barbuto; G R Lee
Journal:  J Clin Invest       Date:  1976-11       Impact factor: 14.808

10.  Red-cell uroporphyrinogen decarboxylase activity in porphyria cutanea tarda and in other forms of porphyria.

Authors:  B F Felsher; M E Norris; J C Shih
Journal:  N Engl J Med       Date:  1978-11-16       Impact factor: 91.245

View more
  18 in total

1.  Steady-state levels of uroporphyrinogen decarboxylase mRNA in lymphoblastoid cell lines from patients with familial porphyria cutanea tarda and their relatives.

Authors:  J L Hansen; M A Pryor; J B Kennedy; J P Kushner
Journal:  Am J Hum Genet       Date:  1988-06       Impact factor: 11.025

2.  Hepatoerythropoietic porphyria misdiagnosed as child abuse: cutaneous, arthritic, and hematologic manifestations in siblings with a novel UROD mutation.

Authors:  Julie L Cantatore-Francis; Jessica Cohen-Pfeffer; Manisha Balwani; Philip Kahn; Herbert M Lazarus; Robert J Desnick; Julie V Schaffer
Journal:  Arch Dermatol       Date:  2010-05

3.  The effects in vivo of mutationally modified uroporphyrinogen decarboxylase in different hem12 mutants of baker's yeast (Saccharomyces cerevisiae).

Authors:  A Kurlandzka; T Zoladek; J Rytka; R Labbe-Bois; D Urban-Grimal
Journal:  Biochem J       Date:  1988-07-01       Impact factor: 3.857

4.  Hereditary hepatic porphyria with delta aminolevulinate dehydrase deficiency: immunologic characterization of the non-catalytic enzyme.

Authors:  H de Verneuil; M Doss; N Brusco; C Beaumont; Y Nordmann
Journal:  Hum Genet       Date:  1985       Impact factor: 4.132

5.  Characterization of a new mutation (R292G) and a deletion at the human uroporphyrinogen decarboxylase locus in two patients with hepatoerythropoietic porphyria.

Authors:  H de Verneuil; F Bourgeois; F de Rooij; P D Siersema; J H Wilson; B Grandchamp; Y Nordmann
Journal:  Hum Genet       Date:  1992-07       Impact factor: 4.132

Review 6.  Porphyria Diagnostics-Part 1: A Brief Overview of the Porphyrias.

Authors:  Vaithamanithi-Mudumbai Sadagopa Ramanujam; Karl Elmo Anderson
Journal:  Curr Protoc Hum Genet       Date:  2015-07-01

7.  Uroporphyrinogen decarboxylase: complete human gene sequence and molecular study of three families with hepatoerythropoietic porphyria.

Authors:  M J Moran-Jimenez; C Ged; M Romana; R Enriquez De Salamanca; A Taïeb; G Topi; L D'Alessandro; H de Verneuil
Journal:  Am J Hum Genet       Date:  1996-04       Impact factor: 11.025

8.  Mechanistic studies of the inhibition of hepatic uroporphyrinogen decarboxylase in C57BL/10 mice by iron-hexachlorobenzene synergism.

Authors:  A G Smith; J E Francis; S J Kay; J B Greig; F P Stewart
Journal:  Biochem J       Date:  1986-09-15       Impact factor: 3.857

9.  An unhappy triad: hemochromatosis, porphyria cutanea tarda and hepatocellular carcinoma-a case report.

Authors:  Martina-T Mogl; Andreas Pascher; Sabine-J Presser; Michael Schwabe; Peter Neuhaus; Natascha-C Nuessler
Journal:  World J Gastroenterol       Date:  2007-04-07       Impact factor: 5.742

10.  Assignment of human uroporphyrinogen decarboxylase (URO-D) to the p34 band of chromosome 1.

Authors:  A Dubart; M G Mattei; N Raich; D Beaupain; P H Romeo; J F Mattei; M Goossens
Journal:  Hum Genet       Date:  1986-07       Impact factor: 4.132

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.