Literature DB >> 6240403

Neuraminidase deficiency presenting as non-immune hydrops fetalis.

M Beck, S W Bender, H L Reiter, W Otto, R Bässler, H Dancygier, J Gehler.   

Abstract

A newborn infant with oedema, ascites and hepatosplenomegaly is described. In ascites fluid foamy macrophages were found, in a liver biopsy cytoplasmic inclusions and membrane-bound vacuoles were seen. Furthermore the child excreted excessive amounts of sialic acid-rich oligosaccharides in the urine, and therefore a neurovisceral degenerative disorder was assumed. The diagnosis of sialidosis was confirmed by enzymatic assay in cultured fibroblasts, in which a complete deficiency of the lysosomal enzyme neuraminidase could be demonstrated. After recurrent septicaemias the child became dystrophic and died at the age of 6 months. Our case is compared with sialidosis observed by other authors, the wide phenotypic diversity within this biochemical defect is emphasised. The occurrence of hydrops fetalis in lysosomal storage diseases is discussed.

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Year:  1984        PMID: 6240403     DOI: 10.1007/bf00445802

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  23 in total

Review 1.  Sialidosis: a review of human neuraminidase deficiency.

Authors:  J A Lowden; J S O'Brien
Journal:  Am J Hum Genet       Date:  1979-01       Impact factor: 11.025

2.  Rh factor: prevention of isoimmunization and clinical trial on mothers.

Authors:  V J Freda; J G Gorman; W Pollack
Journal:  Science       Date:  1966-02-18       Impact factor: 47.728

3.  Macular cherry-red spots and myoclonus with dementia: coexistent neuraminidase and beta-galactosidase deficiencies.

Authors:  D A Wenger; T J Tarby; C Wharton
Journal:  Biochem Biophys Res Commun       Date:  1978-05-30       Impact factor: 3.575

4.  Differential diagnosis of hydrops fetalis.

Authors:  G A Machin
Journal:  Am J Med Genet       Date:  1981

5.  GM1 gangliosidosis presenting as neonatal ascites.

Authors:  K I Abu-Dalu; H Tamary; N Livni; A I Rivkind; S Yatziv
Journal:  J Pediatr       Date:  1982-06       Impact factor: 4.406

6.  Prenatal diagnosis of sialidosis with combined neuraminidase and beta-galactosidase deficiency.

Authors:  W J Kleijer; A Hoogeveen; F W Verheijen; M F Niermeijer; H Galjaard; J S O'Brien; T G Warner
Journal:  Clin Genet       Date:  1979-07       Impact factor: 4.438

7.  A severe infantile sialidosis: clinical, biochemical, and microscopic features.

Authors:  A S Aylsworth; G H Thomas; J L Hood; N Malouf; J Libert
Journal:  J Pediatr       Date:  1980-04       Impact factor: 4.406

8.  Mucopolysaccharidosis VII (beta-glucuronidase deficiency) presenting as nonimmune hydrops fetalis.

Authors:  A Nelson; L Peterson; B Frampton; W S Sly
Journal:  J Pediatr       Date:  1982-10       Impact factor: 4.406

9.  Simple laboratory determination of excess oligosacchariduria.

Authors:  A C Sewell
Journal:  Clin Chem       Date:  1981-02       Impact factor: 8.327

10.  Generalized N-acetylneuraminic acid storage disease: quantitation and identification of the monosaccharide accumulating in brain and other tissues.

Authors:  L W Hancock; M M Thaler; A L Horwitz; G Dawson
Journal:  J Neurochem       Date:  1982-03       Impact factor: 5.372

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  10 in total

Review 1.  Lysosomal storage disorders in the newborn.

Authors:  Orna Staretz-Chacham; Tess C Lang; Mary E LaMarca; Donna Krasnewich; Ellen Sidransky
Journal:  Pediatrics       Date:  2009-04       Impact factor: 7.124

Review 2.  Type II sialidosis: review of the clinical spectrum and identification of a new splicing defect with chitotriosidase assessment in two patients.

Authors:  A Caciotti; M Di Rocco; M Filocamo; S Grossi; F Traverso; A d'Azzo; C Cavicchi; A Messeri; R Guerrini; E Zammarchi; M A Donati; Amelia Morrone
Journal:  J Neurol       Date:  2009-07-01       Impact factor: 4.849

Review 3.  Screening for lysosomal disorders.

Authors:  K Ullrich
Journal:  Eur J Pediatr       Date:  1994       Impact factor: 3.183

4.  Foamy changes of placental cells in probable beta glucuronidase deficiency associated with hydrops fetalis.

Authors:  J Nelson; B Kenny; D O'Hara; A Harper; D Broadhead
Journal:  J Clin Pathol       Date:  1993-04       Impact factor: 3.411

Review 5.  Primary (genetic) cardiomyopathies in infancy. A survey of possible disorders and guidelines for diagnosis.

Authors:  A Kohlschütter; G Hausdorf
Journal:  Eur J Pediatr       Date:  1986-12       Impact factor: 3.183

6.  Colour Doppler imaging of intracranial vasculopathy in severe infantile sialidosis.

Authors:  M Ries; K H Deeg; D Wölfel; H Ibel; B Maier; G Buheitel
Journal:  Pediatr Radiol       Date:  1992

7.  Type 1 sialidosis presenting with ataxia, seizures and myoclonus with no visual involvement.

Authors:  Ahmed N Mohammad; Katelyn A Bruno; S Hines; Paldeep S Atwal
Journal:  Mol Genet Metab Rep       Date:  2018-01-12

Review 8.  Lysosomal storage disorder in non-immunological hydrops fetalis (NIHF): more common than assumed? Report of four cases with transient NIHF and a review of the literature.

Authors:  Catharina Whybra; Eugen Mengel; Alexandra Russo; Franz Bahlmann; Christoph Kampmann; Michael Beck; Elke Eich; Eva Mildenberger
Journal:  Orphanet J Rare Dis       Date:  2012-11-08       Impact factor: 4.123

9.  Parental Whole-Exome Sequencing Enables Sialidosis Type II Diagnosis due to an NEU1 Missense Mutation as an Underlying Cause of Nephrotic Syndrome in the Child.

Authors:  Reza Maroofian; Isabel Schuele; Maryam Najafi; Zeineb Bakey; Abolfazl Rad; Dinu Antony; Haleh Habibi; Miriam Schmidts
Journal:  Kidney Int Rep       Date:  2018-07-29

Review 10.  Sialidosis: A Review of Morphology and Molecular Biology of a Rare Pediatric Disorder.

Authors:  Aiza Khan; Consolato Sergi
Journal:  Diagnostics (Basel)       Date:  2018-04-25
  10 in total

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