Literature DB >> 6235771

Clinical and genetic variations in the syndrome of adult GM2 gangliosidosis resulting from hexosaminidase A deficiency.

Z Argov, R Navon.   

Abstract

Six patients from three families developed adult GM2 gangliosidosis resulting from severe beta-hexosaminidase A deficiency. The clinical picture varied between and within families and included spinocerebellar, various motor neuron, and cerebellar connection syndromes. Psychosis appeared in each family. Involvement of three generations was recorded in one family. The phenotype of adult GM2 gangliosidosis is variable and cannot form a basis for genetic classification. Detailed hexosaminidase determinations in eight patients from five families revealed all patients to have minor quantities of hexosaminidase A (about 15% of normal), with marked increase in hexosaminidase I isozyme.

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Year:  1984        PMID: 6235771     DOI: 10.1002/ana.410160105

Source DB:  PubMed          Journal:  Ann Neurol        ISSN: 0364-5134            Impact factor:   10.422


  25 in total

1.  Adult onset motor neuron disease: worldwide mortality, incidence and distribution since 1950.

Authors:  A M Chancellor; C P Warlow
Journal:  J Neurol Neurosurg Psychiatry       Date:  1992-12       Impact factor: 10.154

2.  MR imaging and proton spectroscopy of neuronal injury in late-onset GM2 gangliosidosis.

Authors:  Matilde Inglese; Annette O Nusbaum; Gregory M Pastores; John Gianutsos; Edwin H Kolodny; Oded Gonen
Journal:  AJNR Am J Neuroradiol       Date:  2005-09       Impact factor: 3.825

Review 3.  The natural history of juvenile or subacute GM2 gangliosidosis: 21 new cases and literature review of 134 previously reported.

Authors:  Gustavo H B Maegawa; Tracy Stockley; Michael Tropak; Brenda Banwell; Susan Blaser; Fernando Kok; Roberto Giugliani; Don Mahuran; Joe T R Clarke
Journal:  Pediatrics       Date:  2006-10-02       Impact factor: 7.124

4.  Neurophysiological study in chronic GM2 gangliosidosis (hexosaminidase A and B deficiency), with motor neuron disease phenotype.

Authors:  M Mondelli; A Rossi; S Palmeri; N Rizzuto; A Federico
Journal:  Ital J Neurol Sci       Date:  1989-08

5.  Frequency of hexosaminidase A variant alleles among Ashkenazi Jews and prenatal diagnosis of GM2 gangliosidosis.

Authors:  R Navon; A Adam
Journal:  Am J Hum Genet       Date:  1985-09       Impact factor: 11.025

6.  Hexosaminidase A deficiency presenting as juvenile progressive dystonia.

Authors:  R J Hardie; E P Young; J A Morgan-Hughes
Journal:  J Neurol Neurosurg Psychiatry       Date:  1988-03       Impact factor: 10.154

7.  Glycosphingolipids are modulators of disease pathogenesis in amyotrophic lateral sclerosis.

Authors:  James C Dodge; Christopher M Treleaven; Joshua Pacheco; Samantha Cooper; Channa Bao; Marissa Abraham; Mandy Cromwell; S Pablo Sardi; Wei-Lien Chuang; Richard L Sidman; Seng H Cheng; Lamya S Shihabuddin
Journal:  Proc Natl Acad Sci U S A       Date:  2015-06-08       Impact factor: 11.205

Review 8.  Genetic convergence of Parkinson's disease and lysosomal storage disorders.

Authors:  Hao Deng; Xiaofei Xiu; Joseph Jankovic
Journal:  Mol Neurobiol       Date:  2014-08-07       Impact factor: 5.590

Review 9.  The neuropsychiatry of inborn errors of metabolism.

Authors:  Mark Walterfang; Olivier Bonnot; Ramon Mocellin; Dennis Velakoulis
Journal:  J Inherit Metab Dis       Date:  2013-05-23       Impact factor: 4.982

10.  GM2-ganglioside metabolism in hexosaminidase A deficiency states: determination in situ using labeled GM2 added to fibroblast cultures.

Authors:  S S Raghavan; A Krusell; J Krusell; T A Lyerla; E H Kolodny
Journal:  Am J Hum Genet       Date:  1985-11       Impact factor: 11.025

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