Literature DB >> 3763152

Lenticular opacities in carriers of Lowe's syndrome.

G W Cibis, J M Waeltermann, C T Whitcraft, R C Tripathi, D J Harris.   

Abstract

Eleven possible and five obligate carriers of Lowe's syndrome from the same pedigree were examined for lens opacities. All of the obligate carriers and 4 of the 11 at risk had lens abnormalities. The lenticular abnormalities consisted of cortical dots of various shapes that increased in number with the age of the carriers in older obligate carriers, subcapsular plaques were common. Because the syndrome is X linked, such lens changes are explainable by the Lyon's hypothesis. When the number of opacities seen in these subjects were compared to those seen in 100 normal control females 10 to 20 years of age, cataractagenic cases such as diabetes, Down's and fetal nuclear opacities excluded, four probable carriers were identified among the eleven possible carriers in the pedigree. These subjects had significantly greater numbers of opacities, similar to those seen in obligate carriers, compared to controls. We conclude that progressive lens changes are present in carriers of Lowe's syndrome and that young carrier females can be identified reliably when they are compared to age-matched controls by modifying the grading system of Brown and Gardner.

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Year:  1986        PMID: 3763152     DOI: 10.1016/s0161-6420(86)33623-6

Source DB:  PubMed          Journal:  Ophthalmology        ISSN: 0161-6420            Impact factor:   12.079


  8 in total

1.  Mapping the gene for X-linked cataracts and microcornea with facial, dental, and skeletal features to Xp22: an appraisal of the Nance-Horan syndrome.

Authors:  R A Lewis
Journal:  Trans Am Ophthalmol Soc       Date:  1989

2.  Lowe oculocerebrorenal syndrome: DNA-based linkage of the gene to Xq24-q26, using tightly linked flanking markers and the correlation to lens examination in carrier diagnosis.

Authors:  C Wadelius; P Fagerholm; U Pettersson; G Annerén
Journal:  Am J Hum Genet       Date:  1989-02       Impact factor: 11.025

3.  Oculocerebrorenal syndrome of Lowe: Survey of ophthalmic presentations and management.

Authors:  Xiaowan Ma; Ke Ning; Sayena Jabbehdari; Philipp P Prosseda; Yang Hu; Ann Shue; Scott R Lambert; Yang Sun
Journal:  Eur J Ophthalmol       Date:  2020-04-27       Impact factor: 2.597

4.  Ascorbic acid and amino acid values in the aqueous humor of a patient with Lowe's syndrome.

Authors:  S Hayasaka; T Yamada; K Nitta; Y Kaji; S Hiraki; K Tachinami; M Matsumoto; S Yamamoto; S Yamamoto
Journal:  Graefes Arch Clin Exp Ophthalmol       Date:  1997-04       Impact factor: 3.117

5.  Tightly linked flanking markers for the Lowe oculocerebrorenal syndrome, with application to carrier assessment.

Authors:  D S Reilly; R A Lewis; D H Ledbetter; R L Nussbaum
Journal:  Am J Hum Genet       Date:  1988-05       Impact factor: 11.025

6.  A novel pathogenic DNA variation in the OCRL1 gene in Lowe syndrome.

Authors:  Enver Şimşek; Tülay Şimşek; Yıldız Dallar; Önder Can; Patrick J Willems
Journal:  J Clin Res Pediatr Endocrinol       Date:  2011-02-23

Review 7.  Lowe syndrome.

Authors:  Mario Loi
Journal:  Orphanet J Rare Dis       Date:  2006-05-18       Impact factor: 4.123

Review 8.  [Genetic examination in cases of congenital cataract].

Authors:  B Lorenz
Journal:  Ophthalmologe       Date:  2007-07       Impact factor: 1.174

  8 in total

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