Literature DB >> 36121619

Progressive transcriptional changes in metabolic genes and altered fatbody homeostasis in Drosophila model of Huntington's disease.

Akanksha Singh1, Namita Agrawal2.   

Abstract

Huntington's disease (HD) is an autosomal-dominant neurodegenerative disorder marked by progressive neuronal atrophy, particularly in striatum and cerebral cortex. Although predominant manifestations of the disease include loss in the triad of motor, cognitive and behavioral capabilities, metabolic dysfunction in patients and HD models are being increasingly recognized. Patients display progressive body weight loss, which aggravates the disease and leads to cachexia in the terminal stages. Using the Drosophila model of HD, we have earlier reported that diseased flies exhibit an atypical pattern of lipid gain and loss with progression along with exhibiting extensive mitochondrial dysfunction, impaired calcium homeostasis and heightened apoptosis in the fatbody. Here, we first monitored the structural changes that abdominal fatbody undergoes with disease progression. Further, we checked the transcriptional changes of key metabolic genes in whole fly as well as genes regulating mitochondrial function, apoptosis, autophagy and calcium homeostasis in the abdominal fatbody. We found extensive alterations in whole-body and fatbody-specific transcriptional profile of the diseased flies, which was in consort with their stage-specific physiological state. Additionally, we also assessed lysosome-mediated autophagy in the fatbody of diseased flies in order to ascertain the mechanisms contributing to fatbody atrophy at the terminal stage. Interestingly, we found elevated autophagy in fatbody of flies throughout disease progression. This study provides new insights into the effect on peripheral metabolism due to degeneration of neurons in the neurodegenerative disease, thereby discerns novel mechanisms leading to cachexia in diseased flies and advocates for the need of managing metabolic dysfunctions in HD.
© 2022. The Author(s), under exclusive licence to Springer Science+Business Media, LLC, part of Springer Nature.

Entities:  

Keywords:  Autophagy; Drosophila; Fatbody; Huntington’s disease; Lipid metabolism; Peripheral defect

Year:  2022        PMID: 36121619     DOI: 10.1007/s11011-022-01078-2

Source DB:  PubMed          Journal:  Metab Brain Dis        ISSN: 0885-7490            Impact factor:   3.655


  25 in total

1.  Abnormalities in the functioning of adipocytes from R6/2 mice that are transgenic for the Huntington's disease mutation.

Authors:  J N Fain; N A Del Mar ; C A Meade; A Reiner; D Goldowitz
Journal:  Hum Mol Genet       Date:  2001-01-15       Impact factor: 6.150

2.  A Drosophila in vivo screen identifies store-operated calcium entry as a key regulator of adiposity.

Authors:  Jens Baumbach; Petra Hummel; Iris Bickmeyer; Katarzyna M Kowalczyk; Martina Frank; Konstantin Knorr; Anja Hildebrandt; Dietmar Riedel; Herbert Jäckle; Ronald P Kühnlein
Journal:  Cell Metab       Date:  2014-02-04       Impact factor: 27.287

Review 3.  Autophagy: Emerging roles in lipid homeostasis and metabolic control.

Authors:  Patricia Christian; Jennifer Sacco; Khosrow Adeli
Journal:  Biochim Biophys Acta       Date:  2012-12-26

4.  Progressive alterations in the hypothalamic-pituitary-adrenal axis in the R6/2 transgenic mouse model of Huntington's disease.

Authors:  Maria Björkqvist; Asa Petersén; Karl Bacos; Jeremy Isaacs; Per Norlén; Joana Gil; Natalija Popovic; Frank Sundler; Gillian P Bates; Sarah J Tabrizi; Patrik Brundin; Hindrik Mulder
Journal:  Hum Mol Genet       Date:  2006-04-13       Impact factor: 6.150

5.  Weight loss in Huntington disease increases with higher CAG repeat number.

Authors:  N A Aziz; J M M van der Burg; G B Landwehrmeyer; P Brundin; T Stijnen; R A C Roos
Journal:  Neurology       Date:  2008-11-04       Impact factor: 9.910

6.  Fine-tuning autophagy maximises lifespan and is associated with changes in mitochondrial gene expression in Drosophila.

Authors:  Ivana Bjedov; Helena M Cochemé; Andrea Foley; Daniela Wieser; Nathaniel S Woodling; Jorge Iván Castillo-Quan; Povilas Norvaisas; Celia Lujan; Jennifer C Regan; Janne M Toivonen; Michael P Murphy; Janet Thornton; Kerri J Kinghorn; Thomas P Neufeld; Filipe Cabreiro; Linda Partridge
Journal:  PLoS Genet       Date:  2020-11-30       Impact factor: 5.917

7.  Nutrition controls mitochondrial biogenesis in the Drosophila adipose tissue through Delg and cyclin D/Cdk4.

Authors:  Claudia Baltzer; Stefanie K Tiefenböck; Mark Marti; Christian Frei
Journal:  PLoS One       Date:  2009-09-09       Impact factor: 3.240

Review 8.  What fuels the fly: Energy metabolism in Drosophila and its application to the study of obesity and diabetes.

Authors:  Nirmalya Chatterjee; Norbert Perrimon
Journal:  Sci Adv       Date:  2021-06-09       Impact factor: 14.957

9.  Reduction of DILP2 in Drosophila triages a metabolic phenotype from lifespan revealing redundancy and compensation among DILPs.

Authors:  Susan Broughton; Nazif Alic; Cathy Slack; Timothy Bass; Tomoatsu Ikeya; Giovanna Vinti; Anna Maria Tommasi; Yasmine Driege; Ernst Hafen; Linda Partridge
Journal:  PLoS One       Date:  2008-11-13       Impact factor: 3.240

10.  Altered lipid metabolism in Drosophila model of Huntington's disease.

Authors:  Kumari Aditi; Mallikarjun N Shakarad; Namita Agrawal
Journal:  Sci Rep       Date:  2016-08-10       Impact factor: 4.379

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.