Literature DB >> 35468891

Finger trembling improvement after surgery in Hirayama disease: a case report.

Nobuaki Tadokoro1,2, Kyuichi Hashimoto3, Katsuhito Kiyasu4, Yusuke Kasai3, Naoki Aoyama4, Ryuichi Takemasa4, Masahiko Ikeuchi4.   

Abstract

INTRODUCTION: Finger trembling is a characteristic physical finding in Hirayama disease. Although conservative treatment is recommended to stop disease progression, surgery is optional in some cases. However, the postoperative recovery of finger trembling is scarcely reported. CASE
PRESENTATION: A 26-year-old Japanese female patient whose chief complaint was left finger trembling with active finger extension presented at our hospital. Hand weakness without muscle atrophy of the left arm was observed. MRI showed left-side oriented intramedullary signal change with concomitant cord atrophy at C4-5 and C5-6. The CT myelogram (CTM) on flexion showed anterior cord compression and anterior shift of posterior dura matter from C4 to C6. And CTM on extension showed the resolution of both findings. Electrophysiological studies showed active and chronic neuronal damage and preserved motor neuron pool of hand muscle. Since she had exhibited a gradual aggravation of symptoms over a period of 5 years, she underwent anterior cervical discectomy and fusion after careful assessment of both conservative and surgical treatment. Finger trembling recovered soon after surgery. DISCUSSION: Finger trembling is an unfamiliar physical finding in terms of postoperative recovery prediction. Anterior horn cell impairment is postulated as a cause of finger trembling. Postural restoration of spinal cord shape and cerebrospinal fluid around the cord with preserved neural function could facilitate functional recovery.
© 2022. The Author(s), under exclusive licence to International Spinal Cord Society.

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Year:  2022        PMID: 35468891      PMCID: PMC9038729          DOI: 10.1038/s41394-022-00514-w

Source DB:  PubMed          Journal:  Spinal Cord Ser Cases        ISSN: 2058-6124


  17 in total

1.  Anterior spinal decompression and fusion for cervical flexion myelopathy in young patients.

Authors:  Kei Watanabe; Kazuhiro Hasegawa; Toru Hirano; Naoto Endo; Akiyoshi Yamazaki; Takao Homma
Journal:  J Neurosurg Spine       Date:  2005-08

2.  Severe cervical flexion myelopathy with long tract signs: a case report and a review of literature.

Authors:  Takahito Fujimori; Akiko Tamura; Toshitada Miwa; Motoki Iwasaki; Takenori Oda
Journal:  Spinal Cord Ser Cases       Date:  2017-05-11

3.  C8 and T1 innervation of forearm muscles.

Authors:  Takashi Chiba; Fumie Konoeda; Mana Higashihara; Hisao Kamiya; Chizuko Oishi; Yuki Hatanaka; Masahiro Sonoo
Journal:  Clin Neurophysiol       Date:  2014-08-27       Impact factor: 3.708

4.  [Cervical collar therapy for juvenile muscular atrophy of distal upper extremity (Hirayama disease): results from 38 cases].

Authors:  Y Tokumaru; K Hirayama
Journal:  Rinsho Shinkeigaku       Date:  2001 Apr-May

5.  Spinal kyphosis causes demyelination and neuronal loss in the spinal cord: a new model of kyphotic deformity using juvenile Japanese small game fowls.

Authors:  Kentaro Shimizu; Masaya Nakamura; Yuji Nishikawa; Sadahisa Hijikata; Kazuhiro Chiba; Yoshiaki Toyama
Journal:  Spine (Phila Pa 1976)       Date:  2005-11-01       Impact factor: 3.468

6.  A clinical, magnetic resonance imaging, and survival motor neuron gene deletion study of Hirayama disease.

Authors:  U K Misra; J Kalita; V N Mishra; A Kesari; B Mittal
Journal:  Arch Neurol       Date:  2005-01

7.  Myelopathy hand. New clinical signs of cervical cord damage.

Authors:  K Ono; S Ebara; T Fuji; K Yonenobu; K Fujiwara; K Yamashita
Journal:  J Bone Joint Surg Br       Date:  1987-03

8.  Nationwide survey of juvenile muscular atrophy of distal upper extremity (Hirayama disease) in Japan.

Authors:  Kunio Tashiro; Seiji Kikuchi; Yasuo Itoyama; Yukio Tokumaru; Gen Sobue; Eiichiro Mukai; Ichiro Akiguchi; Kenji Nakashima; Jun-ichi Kira; Keizo Hirayama
Journal:  Amyotroph Lateral Scler       Date:  2006-03

9.  Minipolymyoclonus: A Critical Appraisal.

Authors:  Jacky Ganguly; Jia Ren Chai; Mandar Jog
Journal:  J Mov Disord       Date:  2021-05-26
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