Literature DB >> 35195872

Clinical exome sequencing uncovers an unsuspected diagnosis of Bartter syndrome type 2 in a child with incidentally detected nephrocalcinosis.

Anshuman Saha1, Priyadarshini Pande2, Kinnari Vala3, Shahenaz Kapadia3, Himanshu Patel3.   

Abstract

Nephrocalcinosis is a characteristic feature of both type 1 and type 2 Bartter syndrome. Bartter syndrome type 2 presents antenatally and very early in life. Late-onset presentation with isolated nephrocalcinosis is extremely rare. We describe an 11-year-old girl with incidentally detected medullary nephrocalcinosis on renal ultrasonography. She was clinically suspected to have primary hyperoxaluria based on high urine oxalate. However, clinical exome sequencing revealed a pathogenic missense variant in the KCNJ1 gene leading to the molecular diagnosis of Bartter syndrome type 2. Both parents were heterozygous carriers of the same variant. Subsequent investigations did reveal a mild Bartter syndrome phenotype with mild metabolic alkalosis, high urine chloride and high renin and aldosterone. Our case illustrates phenotypic heterogeneity of Bartter syndrome type 2 and the usefulness of genetic testing in establishing the correct diagnosis and guiding further management in such cases.
© 2022. The Author(s) under exclusive licence to The Japan Society of Nephrology.

Entities:  

Keywords:  Bartter syndrome type 2; Clinical exome sequencing; KCNJ1 mutation; Nephrocalcinosis

Year:  2022        PMID: 35195872     DOI: 10.1007/s13730-022-00694-2

Source DB:  PubMed          Journal:  CEN Case Rep        ISSN: 2192-4449


  1 in total

1.  Nephrocalcinosis as adult presentation of Bartter syndrome type II.

Authors:  L Huang; G P M Luiken; I C van Riemsdijk; F Petrij; A A M Zandbergen; A Dees
Journal:  Neth J Med       Date:  2014-02       Impact factor: 1.422

  1 in total

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