Literature DB >> 35103203

Atheromatosis of the Scalp: A Novel Feature of Chronic Progressive External Ophthalmoplegia Plus Due to a Single Mitochondrial DNA Deletion.

Josef Finsterer1.   

Abstract

Chronic progressive external ophthalmoplegia (CPEO) manifests phenotypically as ptosis with ophthalmoplegia or CPEO-plus, with the affection of muscles or organs other than the extra-ocular eye muscles. Herein, a case of CPEO-plus caused by a single mitochondrial DNA (mtDNA) deletion is represented, along with several previously unreported phenotypic features. The patient is a 76-year-old Caucasian female who had experienced slowly progressive bilateral ptosis since the age of 15, followed by gradual ophthalmoparesis without double vision. Since the age of 56, she had developed mild quadriparesis, depression, easy fatigability, hypersomnia, a facial tic, optic atrophy, cataract, glaucoma, hepatomegaly, hepatic steatosis, cholecystolithiasis, diverticulosis, hyperhidrosis, mild hyper-creatine-kinase-emia, hyperlipidemia, and hyperuricemia. Moreover, she had faced previously unreported manifestations of mitochondrial disorders, psoriasis, and multiple scalp atheromas. The phenotype and a single 5kb mtDNA deletion were employed to diagnose CPEO-plus. This case demonstrates that the phenotypic spectrum of CPEO-plus is broader than expected, that psoriasis and scalp atheromas are unique features of a mitochondrial disorder, and that CPEO progresses to CPEO-plus during the years.
Copyright © 2021, Finsterer et al.

Entities:  

Keywords:  atheroma; deletion; mitochondrial; mtdna; multisystem; ophthalmoplegia; phenotype; phenotypic heterogeneity; psoriasis; respiratory chain

Year:  2021        PMID: 35103203      PMCID: PMC8783651          DOI: 10.7759/cureus.20641

Source DB:  PubMed          Journal:  Cureus        ISSN: 2168-8184


  21 in total

1.  Compensatory amplification of mtDNA in a patient with a novel deletion/duplication and high mutant load.

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2.  Novel POLG mutation in a patient with early-onset parkinsonism, progressive external ophthalmoplegia and optic atrophy.

Authors:  Lin Ma; Wei Mao; Erhe Xu; Yanning Cai; Chaodong Wang; Jagadish K Chhetri; Piu Chan
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4.  External ophthalmoplegia with severe progressive multiorgan involvement associated with the mtDNA A3243G mutation.

Authors:  Sun Hansrote; Sidney Croul; Mary Selak; Bernadette Kalman; Robert J Schwartzman
Journal:  J Neurol Sci       Date:  2002-05-15       Impact factor: 3.181

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Journal:  No To Shinkei       Date:  1993-08

Review 6.  Mitochondrial depletion syndromes in children and adults.

Authors:  Josef Finsterer; Uwe Ahting
Journal:  Can J Neurol Sci       Date:  2013-09       Impact factor: 2.104

7.  Adult mitochondrial DNA depletion syndrome with mild manifestations.

Authors:  Josef Finsterer; Gabor G Kovacs; Uwe Ahting
Journal:  Neurol Int       Date:  2013-06-25

8.  A novel mitochondrial tRNA(Ala) gene variant causes chronic progressive external ophthalmoplegia in a patient with Huntington disease.

Authors:  Massimiliano Filosto; Gaetana Lanzi; Claudia Nesti; Valentina Vielmi; Eleonora Marchina; Anna Galvagni; Silvia Giliani; Filippo M Santorelli; Alessandro Padovani
Journal:  Mol Genet Metab Rep       Date:  2016-02-27

9.  Mitochondrial tRNA mutations in Chinese Children with Tic Disorders.

Authors:  Peifang Jiang; Yinjie Ling; Tao Zhu; Xiaoying Luo; Yilin Tao; Feilong Meng; Weixin Cheng; Yanchun Ji
Journal:  Biosci Rep       Date:  2020-12-08       Impact factor: 3.840

Review 10.  Clinicogenetical Variants of Progressive External Ophthalmoplegia - An Especial Review of Non-ophthalmic Manifestations.

Authors:  Mehdi Maghbooli; Majid Ghaffarpour; Taher Ghazizadeh; Nazanin Azizi Shalbaf; Ghazal MalekMahmoudi
Journal:  Neurol India       Date:  2020 Jul-Aug       Impact factor: 2.117

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