| Literature DB >> 34651299 |
Thibault Comont1, Mael Heiblig2, Etienne Rivière3, Louis Terriou4, Julien Rossignol5, Didier Bouscary6, Virginie Rieu7, Guillaume Le Guenno7, Alexis Mathian8, Achille Aouba9, Julien Vinit10, Jeremie Dion1, Olivier Kosmider11, Benjamin Terrier12, Sophie Georgin-Lavialle13, Pierre Fenaux14, Arsène Mekinian15.
Abstract
Azacitidine can be effective in myelodysplastic syndromes (MDS) associated with inflammatory/autoimmune diseases. Vacuoles, E1 Enzyme, X-linked, Autoinflammatory, Somatic syndrome (VEXAS) is a new monogenic autoinflammatory syndrome caused by somatic ubiquitin-like modifier-activating enzyme 1 (UBA1) mutation, often associated with MDS, whose treatment is difficult and not yet codified. Based on a French nationwide registry of 116 patients with VEXAS, we report the efficacy and safety of azacitidine treatment in 11 patients with VEXAS with MDS. Clinical response of VEXAS to azacitidine was achieved in five patients (46%), during 6, 8+, 12, 21, 27+ months respectively, suggesting that azacitidine can be effective in selected patients with VEXAS and associated MDS.Entities:
Keywords: VEXAS syndrome; azacitidine; myelodysplastic syndrome
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Year: 2021 PMID: 34651299 DOI: 10.1111/bjh.17893
Source DB: PubMed Journal: Br J Haematol ISSN: 0007-1048 Impact factor: 6.998