Literature DB >> 3456164

Deficiency of adenosine deaminase in the wasted mouse.

C M Abbott, C J Skidmore, A G Searle, J Peters.   

Abstract

Wasted (wst) is a spontaneous mutation with autosomal recessive inheritance. Abnormally low levels of adenosine deaminase have been found in erythrocytes from the wasted mouse. Enzyme activity in wst/wst mice is reduced to 38% of that found in the erythrocytes from control mice, and the apparent Km for adenosine is reduced to 51% of control. These changes imply an alteration in the catalytic properties of the enzyme arising from a change in the primary structure of the protein. We postulate that wasted is a mutation in the structural gene for adenosine deaminase. In man, the autosomal recessive form of severe combined immunodeficiency is associated, in about one-third of cases, with a deficiency of adenosine deaminase. Wasted mice are immunodeficient, develop neurological abnormalities, and die soon after weaning. These features are shared with the human syndrome. We therefore further suggest that the wasted mouse is an animal model for this form of severe combined immunodeficiency that will have potential use in gene-therapy studies.

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Year:  1986        PMID: 3456164      PMCID: PMC322930          DOI: 10.1073/pnas.83.3.693

Source DB:  PubMed          Journal:  Proc Natl Acad Sci U S A        ISSN: 0027-8424            Impact factor:   11.205


  14 in total

1.  A rapid and sensitive method for the quantitation of microgram quantities of protein utilizing the principle of protein-dye binding.

Authors:  M M Bradford
Journal:  Anal Biochem       Date:  1976-05-07       Impact factor: 3.365

2.  Studies of the relationship between adenosine deaminase and immune function.

Authors:  P W Burridge; V Paetkau; J F Henderson
Journal:  J Immunol       Date:  1977-08       Impact factor: 5.422

3.  Adenosine-deaminase deficiency in two patients with severely impaired cellular immunity.

Authors:  E R Giblett; J E Anderson; F Cohen; B Pollara; H J Meuwissen
Journal:  Lancet       Date:  1972-11-18       Impact factor: 79.321

4.  Regional assignment of ADA and ITPA to mouse chromosome 2 (C1----ter). A demonstration of the conserved linkage of enzyme and proto-oncogene loci.

Authors:  M J Siciliano; R E Fournier; R L Stallings
Journal:  J Hered       Date:  1984 May-Jun       Impact factor: 2.645

5.  Amerioration of neurologic abnormalities after "enzyme replacement" in adenosine deaminase deficiency.

Authors:  R Hirschhorn; P S Paageorgiou; H H Kesarwala; L T Taft
Journal:  N Engl J Med       Date:  1980-08-14       Impact factor: 91.245

Review 6.  Biochemistry of diseases of immunodevelopment.

Authors:  D W Martin; E W Gelfand
Journal:  Annu Rev Biochem       Date:  1981       Impact factor: 23.643

7.  'Wasted', a new mutant of the mouse with abnormalities characteristic to ataxia telangiectasia.

Authors:  L D Shultz; H O Sweet; M T Davisson; D R Coman
Journal:  Nature       Date:  1982-06-03       Impact factor: 49.962

8.  Developmental changes of adenosine deaminase, xanthine oxidase, and uricase in mouse tissues.

Authors:  P C Lee
Journal:  Dev Biol       Date:  1973-04       Impact factor: 3.582

9.  Adenosine deaminase (ADA) deficiency in cells derived from humans with severe combined immunodeficiency is due to an aberration of the ADA protein.

Authors:  D Valerio; M G Duyvesteyn; H van Ormondt; P Meera Khan; A J van der Eb
Journal:  Nucleic Acids Res       Date:  1984-01-25       Impact factor: 16.971

10.  Further data on the adenosine deaminase (ADA) polymprphism and a report of a new phenotype.

Authors:  D A Hopkinson; P J Cook; H Harris
Journal:  Ann Hum Genet       Date:  1969-05       Impact factor: 1.670

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  3 in total

1.  Localization of the inosine triphosphatase locus (Itp) on chromosome 2 of the mouse.

Authors:  B A Taylor; D M Walls; M J Wimsatt
Journal:  Biochem Genet       Date:  1987-04       Impact factor: 1.890

2.  Adenosine deaminase, Ada, is in mouse chromosome 2H3, and is not allelic with wasted, wst.

Authors:  C M Abbott; E P Evans; M Burtenshaw; S T Ball; C J Skidmore; J Jones; J Peters
Journal:  Biochem Genet       Date:  1991-12       Impact factor: 1.890

3.  Disruption of the adenosine deaminase (ADA) gene using a dicistronic promoterless construct: production of an ADA-deficient homozygote ES cell line.

Authors:  S Vaulont; S Daines; M Evans
Journal:  Transgenic Res       Date:  1995-07       Impact factor: 2.788

  3 in total

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