| Literature DB >> 34310663 |
Jifeng Bian1, Sehun Kim1, Sarah J Kane1, Jenna Crowell1, Julianna L Sun1,2, Jeffrey Christiansen1, Eri Saijo1, Julie A Moreno1, James DiLisio1, Emily Burnett1, Sandra Pritzkow3, Damian Gorski3, Claudio Soto3, Terry J Kreeger4, Aru Balachandran5, Gordon Mitchell5, Michael W Miller6, Romolo Nonno7, Turid Vikøren8, Jørn Våge8, Knut Madslien8, Linh Tran8, Tram Thu Vuong8, Sylvie L Benestad8, Glenn C Telling1,2.
Abstract
Prions are infectious proteins causing fatal, transmissible neurodegenerative diseases of animals and humans. Replication involves template-directed refolding of host encoded prion protein, PrPC, by its infectious conformation, PrPSc. Following its discovery in captive Colorado deer in 1967, uncontrollable contagious transmission of chronic wasting disease (CWD) led to an expanded geographic range in increasing numbers of free-ranging and captive North American (NA) cervids. Some five decades later, detection of PrPSc in free-ranging Norwegian (NO) reindeer and moose marked the first indication of CWD in Europe. To assess the properties of these emergent NO prions and compare them with NA CWD we used transgenic (Tg) and gene targeted (Gt) mice expressing PrP with glutamine (Q) or glutamate (E) at residue 226, a variation in wild type cervid PrP which influences prion strain selection in NA deer and elk. Transmissions of NO moose and reindeer prions to Tg and Gt mice recapitulated the characteristic features of CWD in natural hosts, revealing novel prion strains with disease kinetics, neuropathological profiles, and capacities to infect lymphoid tissues and cultured cells that were distinct from those causing NA CWD. In support of strain variation, PrPSc conformers comprising emergent NO moose and reindeer CWD were subject to selective effects imposed by variation at residue 226 that were different from those controlling established NA CWD. Transmission of particular NO moose CWD prions in mice expressing E at 226 resulted in selection of a kinetically optimized conformer, subsequent transmission of which revealed properties consistent with NA CWD. These findings illustrate the potential for adaptive selection of strain conformers with improved fitness during propagation of unstable NO prions. Their potential for contagious transmission has implications for risk analyses and management of emergent European CWD. Finally, we found that Gt mice expressing physiologically controlled PrP levels recapitulated the lymphotropic properties of naturally occurring CWD strains resulting in improved susceptibilities to emergent NO reindeer prions compared with over-expressing Tg counterparts. These findings underscore the refined advantages of Gt models for exploring the mechanisms and impacts of strain selection in peripheral compartments during natural prion transmission.Entities:
Year: 2021 PMID: 34310663 DOI: 10.1371/journal.ppat.1009748
Source DB: PubMed Journal: PLoS Pathog ISSN: 1553-7366 Impact factor: 6.823