Literature DB >> 34183725

In Silico identification of a common mobile element insertion in exon 4 of RP1.

Dongju Won1, Joo-Yeon Hwang2,3, Yeeun Shim4, Suk Ho Byeon4,5, Junwon Lee6, Christopher Seungkyu Lee5, Min Kim6, Hyun Taek Lim7, Jong Rak Choi1, Seung-Tae Lee8, Jinu Han9.   

Abstract

Mobile element insertions (MEIs) typically exceed the read lengths of short-read sequencing technologies and are therefore frequently missed. Recently, a founder Alu insertion in exon 4 of RP1 has been detected in Japanese patients with macular dystrophy by PCR and gel electrophoresis. We aimed to develop a grep search program for the detection of the Alu insertion in exon 4 of RP1 using unprocessed short reads. Among 494 unrelated Korean patients with inherited eye diseases, 273 patients with specific retinal phenotypes who were previously genotyped by targeted panel or whole exome sequencing were selected. Five probands had a single heterozygous truncating RP1 variant, and one of their unaffected parents also carry this variant. To find a hidden genetic variant, whole genome sequencing was performed in two patients, and it revealed AluY c.4052_4053ins328/p.(Tyr1352Alafs*9) insertion in RP1 exon 4. This AluY insertion was additionally identified in other 3 families, which was confirmed by PCR and gel electrophoresis. We developed simplified grep search program to detect this AluY insertion in RP1 exon 4. The simple grep search revealed a median variant allele frequency of 0.282 (interquartile range, 0.232-0.383), with no false-positive results using 120 control samples. The MEI in RP1 exon 4 was a common founder mutation in Korean, occurring in 1.8% of our cohort. The RP1-Alu grep program efficiently detected the AluY insertion, without the preprocessing of raw data or complex installation processes.

Entities:  

Year:  2021        PMID: 34183725     DOI: 10.1038/s41598-021-92834-4

Source DB:  PubMed          Journal:  Sci Rep        ISSN: 2045-2322            Impact factor:   4.379


  5 in total

1.  Alu-element insertion in an OPA1 intron sequence associated with autosomal dominant optic atrophy.

Authors:  Gian Nicola Gallus; Elena Cardaioli; Alessandra Rufa; Paola Da Pozzo; Silvia Bianchi; Camilla D'Eramo; Michele Collura; Manuela Tumino; Lorenzo Pavone; Antonio Federico
Journal:  Mol Vis       Date:  2010-02-10       Impact factor: 2.367

2.  Biallelic RP1-associated retinal dystrophies: Expanding the mutational and clinical spectrum.

Authors:  Rachel M Huckfeldt; Florin Grigorian; Emily Place; Jason I Comander; Demetrios Vavvas; Lucy H Young; Paul Yang; Maria Shurygina; Eric A Pierce; Mark E Pennesi
Journal:  Mol Vis       Date:  2020-06-03       Impact factor: 2.367

3.  Copy number variations and multiallelic variants in Korean patients with Leber congenital amaurosis.

Authors:  Dongheon Surl; Saeam Shin; Seung-Tae Lee; Jong Rak Choi; Junwon Lee; Suk Ho Byeon; Sueng-Han Han; Hyun Taek Lim; Jinu Han
Journal:  Mol Vis       Date:  2020-02-24       Impact factor: 2.367

4.  Identification of a novel nonsense mutation in RP1 that causes autosomal recessive retinitis pigmentosa in an Indonesian family.

Authors:  Anna M Siemiatkowska; Galuh D N Astuti; Kentar Arimadyo; Anneke I den Hollander; Sultana M H Faradz; Frans P M Cremers; Rob W J Collin
Journal:  Mol Vis       Date:  2012-10-03       Impact factor: 2.367

5.  Diagnostic application of clinical exome sequencing in Leber congenital amaurosis.

Authors:  Jinu Han; John Hoon Rim; In Sik Hwang; Jieun Kim; Saeam Shin; Seung-Tae Lee; Jong Rak Choi
Journal:  Mol Vis       Date:  2017-09-20       Impact factor: 2.367

  5 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.