Literature DB >> 33779789

[Rare bone disorders and respective treatments].

Lothar Seefried1, Franz Jakob2.   

Abstract

Delineating the genetic background and the underlying pathophysiology of rare skeletal dysplasias enables a broader understanding of these disorders as well as novel perspectives regarding differential diagnosis and targeted development of therapeutic approaches. Hypophosphatasia (HPP) due to genetically determined Alkaline Phosphatase deficiency exemplifies this development. While an enzyme replacement therapy could be established for severe HPP with the prevailing bone manifestation, the clinical impact of not immediately bone-related manifestations just being successively understood. Correspondingly, the elucidation of the pathophysiology underlying renal phosphate wasting expanded our knowledge regarding phosphate metabolism and bone health and facilitated the development of an anti-FGF-23 Antibody for targeted treatment of X‑linked Hypophosphatemia (XLH). Evolutions regarding the nosology of osteogenesis imperfecta (OI) along with the identification of further causative genes also detected in the context of genetically determined osteoporosis illustrate the pathophysiologic interrelation between monogenetic bone dysplasias and multifactorial osteoporosis. While current therapeutic strategies for OI follow osteoporosis treatment, the expanding knowledge about OI forms the fundament for establishing improved treatment strategies-for both OI and osteoporosis. Similar developments are emerging regarding rare skeletal disorders like Achondroplasia, Fibrodysplasia ossificans progressive and Morbus Morquio (Mukopolysaccharidosis Type IV).

Entities:  

Keywords:  Genetically determined bone disorders; Hypophosphatasia; Osteogenesis imperfecta; Skeletal dysplasias; X‑linked Hypophosphatemia

Year:  2021        PMID: 33779789     DOI: 10.1007/s00108-021-00995-1

Source DB:  PubMed          Journal:  Internist (Berl)        ISSN: 0020-9554            Impact factor:   0.743


  7 in total

1.  Bone mineral density and fracture risk in adult patients with hypophosphatasia.

Authors:  F Genest; L Claußen; D Rak; L Seefried
Journal:  Osteoporos Int       Date:  2020-09-02       Impact factor: 4.507

2.  Mineral Intake and Clinical Symptoms in Adult Patients with Hypophosphatasia.

Authors:  Katinka Kuehn; Andreas Hahn; Lothar Seefried
Journal:  J Clin Endocrinol Metab       Date:  2020-08-01       Impact factor: 5.958

Review 3.  Osteogenesis imperfecta: an update on clinical features and therapies.

Authors:  Ronit Marom; Brien M Rabenhorst; Roy Morello
Journal:  Eur J Endocrinol       Date:  2020-10       Impact factor: 6.664

4.  Burden of Illness in Adults With Hypophosphatasia: Data From the Global Hypophosphatasia Patient Registry.

Authors:  Lothar Seefried; Kathryn Dahir; Anna Petryk; Wolfgang Högler; Agnès Linglart; Gabriel Ángel Martos-Moreno; Keiichi Ozono; Shona Fang; Cheryl Rockman-Greenberg; Priya S Kishnani
Journal:  J Bone Miner Res       Date:  2020-08-10       Impact factor: 6.741

Review 5.  ADULT HYPOPHOSPHATASIA TREATED WITH TERIPARATIDE: REPORT OF 2 PATIENTS AND REVIEW OF THE LITERATURE.

Authors:  Pauline M Camacho; Alaleh M Mazhari; Cory Wilczynski; Ruth Kadanoff; Steven Mumm; Michael P Whyte
Journal:  Endocr Pract       Date:  2016-04-04       Impact factor: 3.443

6.  Hypophosphatasia: a genetic-based nosology and new insights in genotype-phenotype correlation.

Authors:  Etienne Mornet; Agnès Taillandier; Christelle Domingues; Annika Dufour; Emmanuelle Benaloun; Nicole Lavaud; Fabienne Wallon; Nathalie Rousseau; Carole Charle; Mihelaiti Guberto; Christine Muti; Brigitte Simon-Bouy
Journal:  Eur J Hum Genet       Date:  2020-09-24       Impact factor: 4.246

  7 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.