Literature DB >> 33603644

Chronic Exposure to Cadmium and Antioxidants Does Not Affect the Dynamics of Expanded CAG•CTG Trinucleotide Repeats in a Mouse Cell Culture System of Unstable DNA.

Mário Gomes-Pereira1, Darren G Monckton2.   

Abstract

More than 30 human disorders are caused by the expansion of simple sequence DNA repeats, among which triplet repeats remain the most frequent. Most trinucleotide repeat expansion disorders affect primarily the nervous system, through mechanisms of neurodysfunction and/or neurodegeneration. While trinucleotide repeat tracts are short and stably transmitted in unaffected individuals, disease-associated expansions are highly dynamic in the germline and in somatic cells, with a tendency toward further expansion. Since longer repeats are associated with increasing disease severity and earlier onset of symptoms, intergenerational repeat size gains account for the phenomenon of anticipation. In turn, higher levels of age-dependent somatic expansion have been linked with increased disease severity and earlier age of onset, implicating somatic instability in the onset and progression of disease symptoms. Hence, tackling the root cause of symptoms through the control of repeat dynamics may provide therapeutic modulation of clinical manifestations. DNA repair pathways have been firmly implicated in the molecular mechanism of repeat length mutation. The demonstration that repeat expansion depends on functional DNA mismatch repair (MMR) proteins, points to MMR as a potential therapeutic target. Similarly, a role of DNA base excision repair (BER) in repeat expansion has also been suggested, particularly during the removal of oxidative lesions. Using a well-characterized mouse cell model system of an unstable CAGCTG trinucleotide repeat, we tested if expanded repeat tracts can be stabilized by small molecules with reported roles in both pathways: cadmium (an inhibitor of MMR activity) and a variety of antioxidants (capable of neutralizing oxidative species). We found that chronic exposure to sublethal doses of cadmium and antioxidants did not result in significant reduction of the rate of trinucleotide repeat expansion. Surprisingly, manganese yielded a significant stabilization of the triplet repeat tract. We conclude that treatment with cadmium and antioxidants, at doses that do not interfere with cell survival and cell culture dynamics, is not sufficient to modify trinucleotide repeat dynamics in cell culture.
Copyright © 2021 Gomes-Pereira and Monckton.

Entities:  

Keywords:  antioxidants; cadmium; cell culture model; mismatch repair; oxidative stress; trinucleotide repeat; unstable DNA

Year:  2021        PMID: 33603644      PMCID: PMC7884634          DOI: 10.3389/fncel.2020.606331

Source DB:  PubMed          Journal:  Front Cell Neurosci        ISSN: 1662-5102            Impact factor:   5.505


  65 in total

1.  Manganese substantially alters the dynamics of translesion DNA synthesis.

Authors:  Heather Hays; Anthony J Berdis
Journal:  Biochemistry       Date:  2002-04-16       Impact factor: 3.162

2.  Oxidative stress causes DNA triplet expansion in Huntington's disease mouse embryonic stem cells.

Authors:  Ida Jonson; Rune Ougland; Arne Klungland; Elisabeth Larsen
Journal:  Stem Cell Res       Date:  2013-08-27       Impact factor: 2.020

3.  Somatic instability of CTG repeat in myotonic dystrophy.

Authors:  T Ashizawa; J R Dubel; Y Harati
Journal:  Neurology       Date:  1993-12       Impact factor: 9.910

4.  Targeting of XJB-5-131 to mitochondria suppresses oxidative DNA damage and motor decline in a mouse model of Huntington's disease.

Authors:  Zhiyin Xun; Sulay Rivera-Sánchez; Sylvette Ayala-Peña; James Lim; Helen Budworth; Erin M Skoda; Paul D Robbins; Laura J Niedernhofer; Peter Wipf; Cynthia T McMurray
Journal:  Cell Rep       Date:  2012-11-01       Impact factor: 9.423

5.  DNA methylation and histone acetylation patterns in cultured bovine fibroblasts for nuclear transfer.

Authors:  Angelica M Giraldo; John W Lynn; Megan N Purpera; Robert A Godke; Kenneth R Bondioli
Journal:  Mol Reprod Dev       Date:  2007-12       Impact factor: 2.609

6.  Somatic expansion of the Huntington's disease CAG repeat in the brain is associated with an earlier age of disease onset.

Authors:  Meera Swami; Audrey E Hendricks; Tammy Gillis; Tiffany Massood; Jayalakshmi Mysore; Richard H Myers; Vanessa C Wheeler
Journal:  Hum Mol Genet       Date:  2009-05-23       Impact factor: 6.150

7.  Mismatch repair genes Mlh1 and Mlh3 modify CAG instability in Huntington's disease mice: genome-wide and candidate approaches.

Authors:  Ricardo Mouro Pinto; Ella Dragileva; Andrew Kirby; Alejandro Lloret; Edith Lopez; Jason St Claire; Gagan B Panigrahi; Caixia Hou; Kim Holloway; Tammy Gillis; Jolene R Guide; Paula E Cohen; Guo-Min Li; Christopher E Pearson; Mark J Daly; Vanessa C Wheeler
Journal:  PLoS Genet       Date:  2013-10-31       Impact factor: 5.917

8.  MSH3 modifies somatic instability and disease severity in Huntington's and myotonic dystrophy type 1.

Authors:  Michael Flower; Vilija Lomeikaite; Marc Ciosi; Sarah Cumming; Fernando Morales; Kitty Lo; Davina Hensman Moss; Lesley Jones; Peter Holmans; Darren G Monckton; Sarah J Tabrizi
Journal:  Brain       Date:  2019-06-19       Impact factor: 13.501

9.  DNA repair pathways underlie a common genetic mechanism modulating onset in polyglutamine diseases.

Authors:  Conceição Bettencourt; Davina Hensman-Moss; Michael Flower; Sarah Wiethoff; Alexis Brice; Cyril Goizet; Giovanni Stevanin; Georgios Koutsis; Georgia Karadima; Marios Panas; Petra Yescas-Gómez; Lizbeth Esmeralda García-Velázquez; María Elisa Alonso-Vilatela; Manuela Lima; Mafalda Raposo; Bryan Traynor; Mary Sweeney; Nicholas Wood; Paola Giunti; Alexandra Durr; Peter Holmans; Henry Houlden; Sarah J Tabrizi; Lesley Jones
Journal:  Ann Neurol       Date:  2016-05-06       Impact factor: 10.422

10.  XJB-5-131-mediated improvement in physiology and behaviour of the R6/2 mouse model of Huntington's disease is age- and sex- dependent.

Authors:  Aris A Polyzos; Nigel I Wood; Paul Williams; Peter Wipf; A Jennifer Morton; Cynthia T McMurray
Journal:  PLoS One       Date:  2018-04-09       Impact factor: 3.240

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.