Literature DB >> 33567613

Genetic Modifiers of Hereditary Neuromuscular Disorders and Cardiomyopathy.

Sholeh Bazrafshan1, Hani Kushlaf2, Mashhood Kakroo1, John Quinlan2, Richard C Becker1, Sakthivel Sadayappan1.   

Abstract

Novel genetic variants exist in patients with hereditary neuromuscular disorders (NMD), including muscular dystrophy. These patients also develop cardiac manifestations. However, the association between these gene variants and cardiac abnormalities is understudied. To determine genetic modifiers and features of cardiac disease in NMD patients, we have reviewed electronic medical records of 651 patients referred to the Muscular Dystrophy Association Care Center at the University of Cincinnati and characterized the clinical phenotype of 14 patients correlating with their next-generation sequencing data. The data were retrieved from the electronic medical records of the 14 patients included in the current study and comprised neurologic and cardiac phenotype and genetic reports which included comparative genomic hybridization array and NGS. Novel associations were uncovered in the following eight patients diagnosed with Limb-girdle Muscular Dystrophy, Bethlem Myopathy, Necrotizing Myopathy, Charcot-Marie-Tooth Disease, Peripheral Polyneuropathy, and Valosin-containing Protein-related Myopathy. Mutations in COL6A1, COL6A3, SGCA, SYNE1, FKTN, PLEKHG5, ANO5, and SMCHD1 genes were the most common, and the associated cardiac features included bundle branch blocks, ventricular chamber dilation, septal thickening, and increased outflow track gradients. Our observations suggest that features of cardiac disease and modifying gene mutations in patients with NMD require further investigation to better characterize genotype-phenotype relationships.

Entities:  

Keywords:  cardiomyopathy; genotype–phenotype relationships; muscular dystrophy; neuromuscular disorders; next-generation sequencing

Year:  2021        PMID: 33567613      PMCID: PMC7915259          DOI: 10.3390/cells10020349

Source DB:  PubMed          Journal:  Cells        ISSN: 2073-4409            Impact factor:   6.600


  64 in total

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Journal:  Nat Genet       Date:  2004-04-04       Impact factor: 38.330

Review 2.  Molecular insights into cardiomyopathies associated with desmin (DES) mutations.

Authors:  Andreas Brodehl; Anna Gaertner-Rommel; Hendrik Milting
Journal:  Biophys Rev       Date:  2018-06-20

3.  Mutations in the human delta-sarcoglycan gene in familial and sporadic dilated cardiomyopathy.

Authors:  S Tsubata; K R Bowles; M Vatta; C Zintz; J Titus; L Muhonen; N E Bowles; J A Towbin
Journal:  J Clin Invest       Date:  2000-09       Impact factor: 14.808

4.  Fukutin gene mutations cause dilated cardiomyopathy with minimal muscle weakness.

Authors:  Terumi Murakami; Yukiko K Hayashi; Satoru Noguchi; Megumu Ogawa; Ikuya Nonaka; Yuzo Tanabe; Mieko Ogino; Fumio Takada; Makoto Eriguchi; Norihiko Kotooka; Kevin P Campbell; Makiko Osawa; Ichizo Nishino
Journal:  Ann Neurol       Date:  2006-11       Impact factor: 10.422

5.  Mitofusin-2 maintains mitochondrial structure and contributes to stress-induced permeability transition in cardiac myocytes.

Authors:  Kyriakos N Papanicolaou; Ramzi J Khairallah; Gladys A Ngoh; Aristide Chikando; Ivan Luptak; Karen M O'Shea; Dushon D Riley; Jesse J Lugus; Wilson S Colucci; W Jonathan Lederer; William C Stanley; Kenneth Walsh
Journal:  Mol Cell Biol       Date:  2011-01-18       Impact factor: 4.272

6.  The coexistence of dynamin 2 mutation and multiple mitochondrial DNA (mtDNA) deletions in the background of severe cardiomyopathy and centronuclear myopathy.

Authors:  Aniko Gal; Gabriella Inczedy-Farkas; Endre Pal; Viktoria Remenyi; Benjamin Bereznai; Laszlo Geller; Zsolt Szelid; Bela Merkely; Maria Judit Molnar
Journal:  Clin Neuropathol       Date:  2015 Mar-Apr       Impact factor: 1.368

7.  Association of dystrophin and an integral membrane glycoprotein.

Authors:  K P Campbell; S D Kahl
Journal:  Nature       Date:  1989-03-16       Impact factor: 49.962

8.  A Nationwide, Population-Based Prevalence Study of Genetic Muscle Disorders.

Authors:  Alice Theadom; Miriam Rodrigues; Gemma Poke; Gina O'Grady; Donald Love; Graeme Hammond-Tooke; Priya Parmar; Ronelle Baker; Valery Feigin; Kelly Jones; Braden Te Ao; Anna Ranta; Richard Roxburgh
Journal:  Neuroepidemiology       Date:  2019-01-18       Impact factor: 3.282

9.  Clinical and molecular studies in a unique family with autosomal dominant limb-girdle muscular dystrophy and Paget disease of bone.

Authors:  V E Kimonis; M J Kovach; B Waggoner; S Leal; A Salam; L Rimer; K Davis; R Khardori; D Gelber
Journal:  Genet Med       Date:  2000 Jul-Aug       Impact factor: 8.822

10.  Identification of the Syrian hamster cardiomyopathy gene.

Authors:  V Nigro; Y Okazaki; A Belsito; G Piluso; Y Matsuda; L Politano; G Nigro; C Ventura; C Abbondanza; A M Molinari; D Acampora; M Nishimura; Y Hayashizaki; G A Puca
Journal:  Hum Mol Genet       Date:  1997-04       Impact factor: 6.150

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  2 in total

1.  Sex differences in the involvement of skeletal and cardiac muscles in myopathic Ano5-/- mice.

Authors:  Steven Foltz; Fang Wu; Nasab Ghazal; Jennifer Q Kwong; H Criss Hartzell; Hyojung J Choo
Journal:  Am J Physiol Cell Physiol       Date:  2022-01-12       Impact factor: 4.249

Review 2.  Mutations in proteins involved in E-C coupling and SOCE and congenital myopathies.

Authors:  Daniela Rossi; Maria Rosaria Catallo; Enrico Pierantozzi; Vincenzo Sorrentino
Journal:  J Gen Physiol       Date:  2022-08-18       Impact factor: 4.000

  2 in total

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