Literature DB >> 33394161

A novel OCT signature in leukemic papillopathy masquerading as autoimmune or infectious uveitis.

Jason M L Miller1, Emily Chang1, Cagri G Besirli1, Mark W Johnson1, Hakan Demirci2,3.   

Abstract

PURPOSE: With therapeutic advances, central nervous system (CNS) involvement in leukemia has become more common. Leukemic optic disc infiltration, often a clinical diagnosis, can present as an isolated finding in primary or relapsed CNS disease and therefore requires early recognition. Not previously well appreciated, we report here signs of intraocular inflammation accompanying leukemic optic disc infiltration, suggesting infectious or non-infectious uveitis as an alternative diagnosis. We describe a novel optical coherence tomography (OCT) sign favoring leukemic infiltration.
METHODS: Retrospective consecutive case series of all leukemic patients with disc edema (5 patients, 6 eyes) presenting to the University of Michigan's Ocular Oncology Clinic between October 2019 and March 2020.
RESULTS: We report five leukemic patients (6 eyes) who were evaluated for disc edema and vitritis and eventually diagnosed with leukemic papillopathy. All five patients initially had a bland lumbar puncture (LP), and all four patients who underwent magnetic resonance imaging (MRI) had no retrobulbar nerve involvement. Clinical findings included preserved visual acuity (n = 5 eyes, 83%), anterior chamber (AC) cell (n = 3 eyes, 50%), vitreous cell (n = 6 eyes, 100%), and retinal whitening (n = 4 eyes, 66%). In five eyes (83%), a diagnosis of infectious or non-infectious uveitis was initially considered. The OCT finding of inner retinal thickening and loss of inner retinal lamination with largely preserved outer retinal architecture helped point towards a leukemic infiltrative process emanating from the disc and spreading retrograde through the nerve fiber layer.
CONCLUSIONS: These cases highlight the difficulty of distinguishing intraocular inflammation associated with leukemic papillopathy from infectious or non-infectious uveitis, especially considering bland LP and negative retrobulbar MRI signal in all our patients. We propose juxtapapillary inner retinal infiltration with the loss of inner retinal lamination and relative preservation of outer retinal architecture on OCT imaging as a finding that supports the diagnosis of leukemic papillopathy.

Entities:  

Keywords:  Infectious uveitis; Leukemia; Leukemic papillopathy; Non-infectious uveitis; Optic neuropathy; Optical coherence tomography (OCT)

Year:  2021        PMID: 33394161     DOI: 10.1007/s00417-020-05055-2

Source DB:  PubMed          Journal:  Graefes Arch Clin Exp Ophthalmol        ISSN: 0721-832X            Impact factor:   3.117


  17 in total

Review 1.  Central nervous system prophylaxis in haematological malignancies.

Authors:  Jeremy Wellwood; K Taylor
Journal:  Intern Med J       Date:  2002 May-Jun       Impact factor: 2.048

2.  Leukaemic infiltration of the optic nerve as the initial manifestation of leukaemic relapse.

Authors:  Y-C Lin; A-G Wang; M-Y Yen; W-M Hsu
Journal:  Eye (Lond)       Date:  2004-05       Impact factor: 3.775

3.  Relapsed T-cell acute lymphoblastic leukaemia in the vitreous of an adult: a case report.

Authors:  R Allchin; A Pradeep; R Sheard; I G Rennie; H S Mudhar
Journal:  Eye (Lond)       Date:  2014-05-09       Impact factor: 3.775

4.  Leukemic involvement of the optic nerve.

Authors:  H Nikaido; H Mishima; H Ono; K Choshi; H Dohy
Journal:  Am J Ophthalmol       Date:  1988-03-15       Impact factor: 5.258

5.  Leukemic infiltration of the optic nerve head.

Authors:  W Ellis; H L Little
Journal:  Am J Ophthalmol       Date:  1973-05       Impact factor: 5.258

6.  Ocular involvement in leukemia--a study of 288 cases.

Authors:  S C Reddy; N Jackson; B S Menon
Journal:  Ophthalmologica       Date:  2003 Nov-Dec       Impact factor: 3.250

7.  Patterns of leukemia incidence in the United States by subtype and demographic characteristics, 1997-2002.

Authors:  Jennifer F Yamamoto; Marc T Goodman
Journal:  Cancer Causes Control       Date:  2007-12-07       Impact factor: 2.506

8.  Ocular relapse in the anterior chamber in childhood acute lymphoblastic leukemia.

Authors:  N Bunin; G Rivera; F Goode; H O Hustu
Journal:  J Clin Oncol       Date:  1987-02       Impact factor: 44.544

9.  Leukemic ophthalmopathy in children.

Authors:  E W Ridgway; N Jaffe; D S Walton
Journal:  Cancer       Date:  1976-10       Impact factor: 6.860

Review 10.  Ocular and orbital involvement in leukemia.

Authors:  M C Kincaid; W R Green
Journal:  Surv Ophthalmol       Date:  1983 Jan-Feb       Impact factor: 6.048

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.