Literature DB >> 33363396

Incidence of HNF1A and GCK MODY Variants in a South African Population.

Tandi E Matsha1, Shanel Raghubeer1, Abegail M Tshivhase1, Saarah F G Davids1, Gloudina M Hon1, Lise Bjørkhaug2, Rajiv T Erasmus1.   

Abstract

BACKGROUND AND AIM: Maturity-onset diabetes of the young (MODY) is the result of single gene variants. To date, fourteen different MODY subtypes have been described. Variants in genes coding for glucokinase (GCK, MODY2) and hepatic nuclear factor 1 alpha (HNF1A, MODY3) are most frequently encountered. MODY patients are often misdiagnosed with type 1 or type 2 diabetes, resulting in incorrect treatment protocols. At the time of reporting, no data are available on MODY prevalence in populations from Africa. Our study aimed to investigate and report on the incidence of MODY-related variants, specifically HNF1A variants, in a population from the Western Cape.
METHODS: Study participants were recruited (1643 in total, 407 males, 1236 females) and underwent anthropometric tests. Thereafter, blood was collected, and real-time PCR was used to screen for specific variants in HNF1A and GCK genes.
RESULTS: Ninety-seven individuals (5.9%) were identified with a specific HNF1A gene polymorphism (rs1169288) and twelve (0.9%) with a GCK polymorphism (rs4607517).
CONCLUSION: In total, 6.6% of the study population expressed MODY variants. To our knowledge, we are the first to report on MODY incidence in Africa. This research provides the basis for MODY incidence studies in South Africa, as well as data on non-Caucasian populations.
© 2020 Matsha et al.

Entities:  

Keywords:  GCK; HNF1A; MODY; South Africa; diabetes mellitus; monogenic diabetes

Year:  2020        PMID: 33363396      PMCID: PMC7754620          DOI: 10.2147/TACG.S281872

Source DB:  PubMed          Journal:  Appl Clin Genet        ISSN: 1178-704X


  24 in total

1.  High frequency of mutations in MODY and mitochondrial genes in Scandinavian patients with familial early-onset diabetes.

Authors:  M Lehto; C Wipemo; S A Ivarsson; C Lindgren; M Lipsanen-Nyman; J Weng; L Wibell; E Widén; T Tuomi; L Groop
Journal:  Diabetologia       Date:  1999-09       Impact factor: 10.122

2.  HNF1alpha controls renal glucose reabsorption in mouse and man.

Authors:  M Pontoglio; D Prié; C Cheret; A Doyen; C Leroy; P Froguel; G Velho; M Yaniv; G Friedlander
Journal:  EMBO Rep       Date:  2000-10       Impact factor: 8.807

Review 3.  Role of molecular genetics in transforming diagnosis of diabetes mellitus.

Authors:  Anders Molven; Pål R Njølstad
Journal:  Expert Rev Mol Diagn       Date:  2011-04       Impact factor: 5.225

4.  Assessment of high-sensitivity C-reactive protein levels as diagnostic discriminator of maturity-onset diabetes of the young due to HNF1A mutations.

Authors:  Katharine R Owen; Gaya Thanabalasingham; Timothy J James; Fredrik Karpe; Andrew J Farmer; Mark I McCarthy; Anna L Gloyn
Journal:  Diabetes Care       Date:  2010-08-19       Impact factor: 17.152

5.  Prevalence, characteristics and clinical diagnosis of maturity onset diabetes of the young due to mutations in HNF1A, HNF4A, and glucokinase: results from the SEARCH for Diabetes in Youth.

Authors:  Catherine Pihoker; Lisa K Gilliam; Sian Ellard; Dana Dabelea; Cralen Davis; Lawrence M Dolan; Carla J Greenbaum; Giuseppina Imperatore; Jean M Lawrence; Santica M Marcovina; Elizabeth Mayer-Davis; Beatriz L Rodriguez; Andrea K Steck; Desmond E Williams; Andrew T Hattersley
Journal:  J Clin Endocrinol Metab       Date:  2013-06-14       Impact factor: 5.958

Review 6.  Diagnosis and management of maturity onset diabetes of the young (MODY).

Authors:  Gaya Thanabalasingham; Katharine R Owen
Journal:  BMJ       Date:  2011-10-19

7.  Systematic Population Screening, Using Biomarkers and Genetic Testing, Identifies 2.5% of the U.K. Pediatric Diabetes Population With Monogenic Diabetes.

Authors:  Maggie Shepherd; Beverley Shields; Suzanne Hammersley; Michelle Hudson; Timothy J McDonald; Kevin Colclough; Richard A Oram; Bridget Knight; Christopher Hyde; Julian Cox; Katherine Mallam; Christopher Moudiotis; Rebecca Smith; Barbara Fraser; Simon Robertson; Stephen Greene; Sian Ellard; Ewan R Pearson; Andrew T Hattersley
Journal:  Diabetes Care       Date:  2016-06-06       Impact factor: 19.112

8.  The development and validation of a clinical prediction model to determine the probability of MODY in patients with young-onset diabetes.

Authors:  B M Shields; T J McDonald; S Ellard; M J Campbell; C Hyde; A T Hattersley
Journal:  Diabetologia       Date:  2012-01-05       Impact factor: 10.122

Review 9.  MODY: history, genetics, pathophysiology, and clinical decision making.

Authors:  Stefan S Fajans; Graeme I Bell
Journal:  Diabetes Care       Date:  2011-08       Impact factor: 19.112

10.  Maturity onset diabetes of the young due to HNF1A variants in Croatia.

Authors:  Tamara Pavić; Agata Juszczak; Edita Pape Medvidović; Carla Burrows; Mario Šekerija; Amanda J Bennett; Jadranka Ćuća Knežević; Anna L Gloyn; Gordan Lauc; Mark I McCarthy; Olga Gornik; Katharine R Owen
Journal:  Biochem Med (Zagreb)       Date:  2018-04-15       Impact factor: 2.313

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