| Literature DB >> 33308940 |
Ali Asghar Okhovat1, Yalda Nilipour2, Reza Boostani3, Fahimeh Vahabizad4, Safa Najmi5, Shahriar Nafissi6, Farzad Fatehi7.
Abstract
Sporadic late-onset nemaline myopathy (SLONM) is a rare, acquired muscle disease presenting with subacute progression in adulthood. It can be accompanied by a monoclonal gammopathy of undetermined significance (MGUS). We describe clinical and histopathological findings of four SLONM patients with MGUS. In all patients, nemaline rod, inter-myofibrillary network disruption, atrophic changes, peripheral basophilic discoloration, vacuole without rim, and cytoplasmic body without inflammation were seen. Three out of four patients were treated with prednisolone in combination with IVIG monthly and had an appropriate response to the treatment. The optimal first-line treatment remains unclear in SLONM-MGUS, although corticosteroids plus IVIg is associated with favorable clinical response. These treatment modalities might be used as an optional treatment before autologous stem cell transplantation; however, further studies with a higher number of patients are required.Entities:
Keywords: Adult; Intravenous immunoglobulins; Monoclonal gammopathy of undetermined significance; Nemaline myopathy; Prednisolone; Therapy
Year: 2020 PMID: 33308940 DOI: 10.1016/j.nmd.2020.11.004
Source DB: PubMed Journal: Neuromuscul Disord ISSN: 0960-8966 Impact factor: 4.296