| Literature DB >> 33301031 |
S Oberbeck1,2,3, A Schrader1,2,3, K Warner1,4, D Jungherz1,2,3, G Crispatzu1,2,3, J von Jan1,2,3, M Chmielewski1,2,3, A Ianevski5, H H Diebner6, P Mayer1,2,3, A Kondo Ados1,2,3, L Wahnschaffe1,2,3, T Braun1,2,3, T A Müller1,2,3, P Wagle2, A Bouska7, T Neumann1,2,3, S Pützer1,2,3, L Varghese1,2,3, N Pflug1, M Thelen1,3, J Makalowski1,3, N Riet1,3, H J M Göx1,2, G Rappl1,3, J Altmüller8, M Kotrová9, T Persigehl10, G Hopfinger11, M L Hansmann4, H Schlößer3, S Stilgenbauer12, J Dürig13, D Mougiakakos14, M von Bergwelt-Baildon15, I Roeder6, S Hartmann4, M Hallek1,2,3, R Moriggl16,17, M Brüggemann9, T Aittokallio5, J Iqbal7, S Newrzela4, H Abken18, M Herling1,2,3.
Abstract
T-cell prolymphocytic leukemia (T-PLL) is a poor-prognostic neoplasm. Differentiation stage and immune-effector functions of the underlying tumor cell are insufficiently characterized. Constitutive activation of the T-cell leukemia 1A (TCL1A) oncogene distinguishes the (pre)leukemic cell from regular postthymic T cells. We assessed activation-response patterns of the T-PLL lymphocyte and interrogated the modulatory impact by TCL1A. Immunophenotypic and gene expression profiles revealed a unique spectrum of memory-type differentiation of T-PLL with predominant central-memory stages and frequent noncanonical patterns. Virtually all T-PLL expressed a T-cell receptor (TCR) and/or CD28-coreceptor without overrepresentation of specific TCR clonotypes. The highly activated leukemic cells also revealed losses of negative-regulatory TCR coreceptors (eg, CTLA4). TCR stimulation of T-PLL cells evoked higher-than-normal cell-cycle transition and profiles of cytokine release that resembled those of normal memory T cells. More activated phenotypes and higher TCL1A correlated with inferior clinical outcomes. TCL1A was linked to the marked resistance of T-PLL to activation- and FAS-induced cell death. Enforced TCL1A enhanced phospho-activation of TCR kinases, second-messenger generation, and JAK/STAT or NFAT transcriptional responses. This reduced the input thresholds for IL-2 secretion in a sensitizer-like fashion. Mice of TCL1A-initiated protracted T-PLL development resembled such features. When equipped with epitope-defined TCRs or chimeric antigen receptors, these Lckpr-hTCL1Atg T cells gained a leukemogenic growth advantage in scenarios of receptor stimulation. Overall, we propose a model of T-PLL pathogenesis in which TCL1A enhances TCR signals and drives the accumulation of death-resistant memory-type cells that use amplified low-level stimulatory input, and whose loss of negative coregulators additionally maintains their activated state. Treatment rationales are provided by combined interception in TCR and survival signaling.Entities:
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Year: 2020 PMID: 33301031 PMCID: PMC7731789 DOI: 10.1182/blood.2019003348
Source DB: PubMed Journal: Blood ISSN: 0006-4971 Impact factor: 22.113