| Literature DB >> 33067680 |
Francesca Granata1, Antonio Toscano2, Enricomaria Mormina3,4, Olimpia Musumeci2, Agostino Tessitore1, Anna Ciranni2, Graziana Tavilla2, Antonio Pitrone1, Sergio Lucio Vinci1, Antonio Armando Caragliano1, Marcello Longo1.
Abstract
Pompe disease is a rare hereditary metabolic disorder caused by α-glucosidase (GAA) deficiency. The late-onset form of the disease (LOPD) is considered a multisystemic disorder which could involve vascular system with cerebrovascular abnormalities such as intracranial aneurysms or dolichoectasia. Intracranial aneurysm rupture may represent a life-threatening emergency. A possible treatment of unruptured intracranial aneurysms (UIAs) should consider both aneurysm-related (aneurysmal size, shape, localization, numbers and hemodynamic factors) and patient-related risk factors (patient's age and sex, hypertension, smoke exposure). Moreover, UIAs management of LOPD patients needs also to take into account the altered blood vessels integrity and elasticity, whose consistency is likely weakened by the deficient GAA activity as a further potential risk factor. We herein present our approach for of UIAs management in three patients with LOPD. Among them, only one patient with a left saccular UIA of the anterior communicating artery, after careful consideration of risk factors, underwent the endovascular treatment. The other two patients were scheduled for a 1-year follow-up, according to radiological, clinical, and risk evaluation features. Finally, we would like to suggest some general recommendations for UIAs management. In particular, if no risk factors are identified, a cautious yearly follow-up is suggested; otherwise, if risk factors are present, endovascular treatment should be considered.Entities:
Keywords: Cerebrovascular disorders; Endovascular treatment; Glycogen storage disease II; Intracranial aneurysm; Pompe disease
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Year: 2020 PMID: 33067680 DOI: 10.1007/s10072-020-04819-2
Source DB: PubMed Journal: Neurol Sci ISSN: 1590-1874 Impact factor: 3.307