Literature DB >> 32712863

A family with an MYH9-related disorder with different phenotypes masquerading as immune thrombocytopaenia: an underreported disorder in Taiwan.

Ying-Chih Huang1, Yu-Hung Shih2, Ching-Yeh Lin2, Ping-Fang Chiu2, Su-Feng Kuo3, Jen-Shiou Lin3, Ming-Ching Shen4,5.   

Abstract

A 66-year-old woman had experienced abnormal bleeding since the age of 7. Thrombocytopenia was not detected until she was 48, and immune thrombocytopenia was diagnosed at age 66. She also reported experiencing hearing disturbance since the age of 30 and acute renal failure since the age of 61 but reported no visual disturbance. Her younger son, who was 40 years old, also experienced abnormal bleeding since the age of 6, but immune thrombocytopenia was diagnosed as late as age 35. He had no other associated disorders. Laboratory examinations of both mother and son revealed a low platelet count (8000 and 29,000 µL, respectively), giant platelets and Döhle body-like granulocyte inclusion bodies. The mother had a high creatinine level (15.4 mg/dL) and normal liver enzyme levels. MYH9 genetic analysis identified a heterozygous mutation, c.101T>A, p.Val34Glu at exon 2 in both patients. These clinical and laboratory findings were consistent with a diagnosis of an MYH9-related disorder with different phenotypes observed in the same family. MYH9-related disorders were recognised in 2003, but were often misdiagnosed as immune thrombocytopenia, and hence, they have rarely been reported in Taiwan.

Entities:  

Keywords:  Immune thrombocytopenia; MYH9; MYH9 mutation; MYH9-related disorder; May–Hegglin anomaly

Mesh:

Substances:

Year:  2020        PMID: 32712863     DOI: 10.1007/s12185-020-02947-1

Source DB:  PubMed          Journal:  Int J Hematol        ISSN: 0925-5710            Impact factor:   2.490


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Authors:  J S Lin; M C Shen; C H Wang; C T Lin
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Journal:  Haematologica       Date:  2004-03       Impact factor: 9.941

4.  A myosin family tree.

Authors:  T Hodge; M J Cope
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  4 in total

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