| Literature DB >> 32572159 |
William Vainchenker1,2,3, Isabelle Plo4,5,6, Mira El-Khoury7,8,9, Xénia Cabagnols7,8,9, Matthieu Mosca7,8,10, Gaëlle Vertenoeil11,12, Christophe Marzac13, Fabrizia Favale14, Olivier Bluteau7,8,10, Florence Lorre14, Amandine Tisserand7,8,9, Graciela Rabadan Moraes7,8,9, Valérie Ugo15, Jean-Christophe Ianotto16, Jerôme Rey17, Eric Solary7,8,10,13, Lydia Roy18, Philippe Rameau8, Najet Debili7,8,10, Florence Pasquier7,8,10,13, Nicole Casadevall7,8,19, Caroline Marty7,8,10, Stefan N Constantinescu11,12,20, Hana Raslova7,8,10.
Abstract
Mutations of calreticulin (CALRm) define a subtype of myeloproliferative neoplasms (MPN). We studied the biological and genetic features of CALR-mutated essential thrombocythemia and myelofibrosis patients. In most cases, CALRm were found in granulocytes, monocytes, B and NK cells, but also in T cells. However, the type 1 CALRm spreads more easily than the type 2 CALRm in lymphoid cells. The CALRm were also associated with an early clonal dominance at the level of hematopoietic stem and progenitor cells (HSPC) with no significant increase during granulo/monocytic differentiation in most cases. Moreover, we found that half of type 2 CALRm patients harbors some homozygous progenitors. Those patients were associated with a higher clonal dominance during granulo/monocytic differentiation than patients with only heterozygous type 2 CALRm progenitors. When associated mutations were present, CALRm were the first genetic event suggesting that they are both the initiating and phenotypic event. In blood, type 1 CALRm led to a greater increased number of all types of progenitors compared with the type 2 CALRm. However, both types of CALRm induced an increase in megakaryocytic progenitors associated with a ruxolitinib-sensitive independent growth and with a mild constitutive signaling in megakaryocytes. At the transcriptional level, type 1 CALRm seems to deregulate more pathways than the type 2 CALRm in megakaryocytes. Altogether, our results show that CALRm modify both the HSPC and megakaryocyte biology with a stronger effect for type 1 than for type 2 CALRm.Entities:
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Year: 2020 PMID: 32572159 DOI: 10.1038/s41388-020-1368-3
Source DB: PubMed Journal: Oncogene ISSN: 0950-9232 Impact factor: 9.867