Literature DB >> 32555393

Unique combination and in silico modeling of biallelic POLR3A variants as a cause of Wiedemann-Rautenstrauch syndrome.

Sehime Gulsun Temel1,2,3, Mahmut Cerkez Ergoren4,5, Elena Manara6, Stefano Paolacci6, Gulten Tuncel4,5, Seref Gul7, Matteo Bertelli8.   

Abstract

Neonatal progeroid syndrome or Wiedemann-Rautenstrauch syndrome (WRS; MIM 264090) is a rare genetic disorder that has clinical symptoms including premature aging, lipodystrophy, and variable mental impairment. Until recently genetic background of the disease was unclear. However, recent studies have indicated that WRS patients have compound heterozygote variations in the POLR3A (RNA polymerase III subunit 3A; MIM 614258) gene that might be responsible for the disease phenotype. In this study we report a WRS patient that has compound heterozygote variations in the POLR3A gene. One of the reported variations in our patient, c.3568C>T, p.(Gln1190Ter), is a novel variation that was not reported before. The other variant, c.3337-11T>C, was previously shown in WRS patients in trans with other variations.

Entities:  

Year:  2020        PMID: 32555393      PMCID: PMC7784914          DOI: 10.1038/s41431-020-0673-1

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  1 in total

1.  PipeMAGI: an integrated and validated workflow for analysis of NGS data for clinical diagnostics.

Authors:  G Marceddu; T Dallavilla; G Guerri; E Manara; P Chiurazzi; M Bertelli
Journal:  Eur Rev Med Pharmacol Sci       Date:  2019-08       Impact factor: 3.507

  1 in total
  1 in total

1.  Distinguishing severe phenotypes associated with pathogenic variants in POLR3A.

Authors:  Stefanie Perrier; Laurence Gauquelin; Jennifer A Wambach; Geneviève Bernard
Journal:  Am J Med Genet A       Date:  2021-11-12       Impact factor: 2.802

  1 in total

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