| Literature DB >> 32436673 |
Patryk Lipiński1, Dorota Jurkiewicz2, Elżbieta Ciara2, Rafał Płoski3, Sabina Więcek4, Anna Bogdańska5, Teresa Stradomska5, Piotr Socha6, Dariusz Rokicki7, Anna Tylki-Szymańska1, Irena Jankowska6.
Abstract
Citrin deficiency can manifest in newborns or infants as neonatal intrahepatic cholestasis caused by citrin deficiency (NICCD). The paper presents a case of Polish NICCD patient presenting with low birth weight, failure to thrive, prolonged cholestatic jaundice with coagulopathy and hypoalbuminemia with normal results of MS/MS newborn screening but with high blood citrulline level observed at 3 months of age. Unreported findings included N-hypoglycosylation and increased serum very-long-chain fatty acids (VLCFA), probably secondary to liver impairment. Final diagnosis was established based on whole-exome sequencing (WES) analysis.Entities:
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Year: 2020 PMID: 32436673 DOI: 10.18388/abp.2020_5202
Source DB: PubMed Journal: Acta Biochim Pol ISSN: 0001-527X Impact factor: 2.349