Literature DB >> 32307446

A highly multiplexed biochemical assay for analytes in dried blood spots: application to newborn screening and diagnosis of lysosomal storage disorders and other inborn errors of metabolism.

Xinying Hong1, Martin Sadilek1, Michael H Gelb2,3.   

Abstract

PURPOSE: To develop a multiplexed assay for the newborn screening of lysosomal storage disorders and additional inborn errors in a flexible, comprehensive, and affordable manner to keep up with the expansion of the newborn screening panel.
METHODS: Ultraperformance liquid chromatography-tandem mass spectrometry (UPLC-MS/MS) was chosen as the detection platform for its superiority compared to traditional flow-injection MS/MS.
RESULTS: A high-throughput, 18-plex UPLC-MS/MS assay was developed for screening purposes with a sample turnaround time of 2.7 minutes. The assay was consolidated such that only four dried blood spot punches were required, and it displayed good precision and reproducibility.
CONCLUSION: We report a highly multiplexed UPLC-MS/MS assay that is appropriate for the newborn screening of 15 lysosomal storage diseases and 3 additional inborn errors. It can be further expanded to include additional conditions for which presymptomatic diagnosis may facilitate optimum treatment outcome.

Entities:  

Keywords:  UPLC-MS/MS; biomarker; enzymatic assay; multiplex; newborn screening

Mesh:

Year:  2020        PMID: 32307446     DOI: 10.1038/s41436-020-0790-9

Source DB:  PubMed          Journal:  Genet Med        ISSN: 1098-3600            Impact factor:   8.822


  3 in total

1.  Multiplex Lysosomal Enzyme Activity Assay on Dried Blood Spots Using Tandem Mass Spectrometry.

Authors:  Hsuan-Chieh Joyce Liao; Hsiao-Jan Chen
Journal:  Methods Mol Biol       Date:  2022

2.  Tandem Mass Spectrometry Enzyme Assays for Multiplex Detection of 10-Mucopolysaccharidoses in Dried Blood Spots and Fibroblasts.

Authors:  Hamid Khaledi; Michael H Gelb
Journal:  Anal Chem       Date:  2020-08-13       Impact factor: 6.986

Review 3.  The rapidly evolving view of lysosomal storage diseases.

Authors:  Giancarlo Parenti; Diego L Medina; Andrea Ballabio
Journal:  EMBO Mol Med       Date:  2021-01-18       Impact factor: 12.137

  3 in total

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