Literature DB >> 32082471

Morphea with Oral Mucosa Involvement and Unilateral Nevoid Telangiectasia as an Early Presentation of Morphea: A Case Report and Review of the Literature.

Penelope Hirt1,2, Suchismita Paul1,2, Weena Phuthongkam1,2, Lawrence Schachner1,2.   

Abstract

Oral mucosal involvement in patients with morphea is quite rare. Unilateral nevoid telangiectasia is a rare vascular dermatosis characterized by unilateral telangiectasia distributed in a dermatomal pattern, especially on the upper trunk and extremities. We describe a case of a 10-year-old female patient that presents with morphea on her left chin and upper lip extending to the inner oral mucosa as well as a unilateral nevoid telangiectasia on her left cheek as an early presentation of localized scleroderma. This case is significant as it demonstrates a striking clinical presentation of morphea and an interesting early presentation of morphea as a unilateral nevoid telangiectasia that improved after treatment with oral methotrexate and prednisone.
Copyright © 2020. Matrix Medical Communications. All rights reserved.

Entities:  

Keywords:  Morphea; localized scleroderma; morphea with oral involvement; nevoid telangiectasia; nevus; telangiectasia

Year:  2020        PMID: 32082471      PMCID: PMC7028378     

Source DB:  PubMed          Journal:  J Clin Aesthet Dermatol        ISSN: 1941-2789


  15 in total

1.  Odontostomatologic involvement in juvenile localised scleroderma of the face.

Authors:  Sabina Trainito; Lorenzo Favero; Giorgia Martini; Thomas Klit Pedersen; Vittorio Favero; Troels Herlin; Francesco Zulian
Journal:  J Paediatr Child Health       Date:  2012-03-12       Impact factor: 1.954

2.  Early localized morphea mimicking an acquired port-wine stain.

Authors:  Rajiv I Nijhawan; Susan Bard; Marianna Blyumin; Aimee C Smidt; Sarah L Chamlin; Elizabeth A Connelly
Journal:  J Am Acad Dermatol       Date:  2010-09-17       Impact factor: 11.527

3.  Unilateral nevoid telangiectasia with no estrogen and progesterone receptors in a pediatric patient.

Authors:  F Sule Afsar; Ragip Ortac; Gulden Diniz
Journal:  Indian J Dermatol Venereol Leprol       Date:  2008 Mar-Apr       Impact factor: 2.545

4.  Unilateral nevoid telangiectasia--report of two cases.

Authors:  Ana Oliveira; Glória Velho; Madalena Sanches; Manuela Selores
Journal:  Int J Dermatol       Date:  2013-03-03       Impact factor: 2.736

5.  Congenital localized scleroderma.

Authors:  Francesco Zulian; Cristina Vallongo; Sheila Knupp Feitosa de Oliveira; Marilynn G Punaro; Joan Ros; Henryka Mazur-Zielinska; Paul Galea; Liviana Da Dalt; Lawrence F Eichenfield
Journal:  J Pediatr       Date:  2006-08       Impact factor: 4.406

6.  A rare cause of gingival recession: morphea with intra-oral involvement.

Authors:  Dominique Van der Veken; Petra De Haes; Esther Hauben; Wim Teughels; Paul Lambrechts
Journal:  Oral Surg Oral Med Oral Pathol Oral Radiol       Date:  2015-02-14

7.  Unilateral dermatomal superficial telangiectasia. Nine new cases and a review of unilateral dermatomal superficial telangiectasia.

Authors:  J K Wilkin; J G Smith; D A Cullison; G E Peters; L J Rodriquez-Rigau; C L Feucht
Journal:  J Am Acad Dermatol       Date:  1983-04       Impact factor: 11.527

8.  A statistical analysis of a pediatric dermatology clinic.

Authors:  L Schachner; N S Ling; S Press
Journal:  Pediatr Dermatol       Date:  1983-10       Impact factor: 1.588

Review 9.  Scleroderma in children: an update.

Authors:  Francesco Zulian; Giorgio Cuffaro; Francesca Sperotto
Journal:  Curr Opin Rheumatol       Date:  2013-09       Impact factor: 5.006

10.  Scleroderma and dentistry: Two case reports.

Authors:  Shantanu Dixit; Chaithra Kalkur; Atul P Sattur; Michael M Bornstein; Fred Melton
Journal:  J Med Case Rep       Date:  2016-10-24
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